Idiopathic Subglottic Stenosis in a Patient with Generalized Port-Wine Stain: A Case Report and Review of Literature

被引:0
作者
Behrangi, Elham [1 ]
Yousefian, Laya [2 ]
Moodi, Aliakbar [3 ]
Azizian, Zahra [1 ]
机构
[1] Iran Univ Med Sci, Rasoul Akram Hosp, Dept Dermatol, Tehran, Iran
[2] Iran Univ Med Sci, Rasoul Akram Hosp, Dept Otolaryngol, Tehran, Iran
[3] Univ Tehran Med Sci, Ziaiyan Hosp, Tehran, Iran
来源
GALEN MEDICAL JOURNAL | 2015年 / 4卷 / 02期
关键词
Port-Wine Stain (PWS); Subglottic Stenosis; Vascular Malformation;
D O I
暂无
中图分类号
R-3 [医学研究方法]; R3 [基础医学];
学科分类号
1001 ;
摘要
Background: Subglottic stenosis is defined as inflammatory narrowing of the airway. It can be related to trauma, intubation, autoimmune disorders, vascular malformations, infection and congenital abnormalities. Pot-Wine Stain (PWS) is a small dermis venous malformation which is present at birth. PWS is found on face and neck, but can occur in throat and can cause subglottic stenosis. Case Report: Authors describe an 18-year-old girl with progressive dyspnea misdiagnosed with asthma having no response to medication. She has no histories of trauma, intubation, gastro-esophageal reflux disease (GERD) or allergy symptoms. Conclusion: Evaluations revealed subglottic stenosis in association with generalized PWS. To the best of our knowledge, this finding has not been reported in English medical literature.
引用
收藏
页码:126 / 128
页数:3
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