RECURRENT ATTACKS OF UNCONSCIOUSNESS WITH DIFFUSE EEG ALPHA-ACTIVITY

被引:8
作者
LOTZ, BP
SCHUTTE, CM
BARTEL, PR
JACOBS, E
机构
[1] UNIV WISCONSIN, DEPT NEUROL, MADISON, WI 53706 USA
[2] UNIV PRETORIA, DEPT NEUROL, PRETORIA, SOUTH AFRICA
来源
SLEEP | 1993年 / 16卷 / 07期
关键词
SLEEP; UNCONSCIOUSNESS; ALPHA-COMA; FLUMAZENIL; GABA;
D O I
10.1093/sleep/16.7.671
中图分类号
R74 [神经病学与精神病学];
学科分类号
摘要
A 45-year-old patient presented with recurrent attacks of unconsciousness, which resembled sleep. However, EEG recordings during these attacks showed diffuse, frontal-dominant 10-Hz alpha activity. Both the attacks and EEG changes reversed promptly with intravenous flumazenil, but not with methylphenidate, atropine or placebo. The attacks could not be prevented with methysergide, flumazenil, clonidine, piracetam or phenytoin. Laboratory investigations revealed a temporal lobe arachnoid cyst, a distal motor and sensory polyneuropathy, abnormal auditory evoked responses during the attack, an abnormal silent period latency and abnormal melatonin regulation. Similar attacks were reported by history in two siblings and in the proband's late father. It is postulated that the attacks of unconsciousness could involve gamma-aminobutyric acid- (GABA-mediated mechanisms.
引用
收藏
页码:671 / 677
页数:7
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