UNUSUAL DENTINAL CHANGES IN DENTINOGENESIS IMPERFECTA ASSOCIATED WITH OSTEOGENESIS IMPERFECTA - A CASE-REPORT

被引：6

作者：

ALDRED, MJ

机构：

[1] Institute of Medical Genetics, University of Wales College of Medicine Cardiff, Wales

来源：

ORAL SURGERY ORAL MEDICINE ORAL PATHOLOGY ORAL RADIOLOGY AND ENDODONTICS | 1992年 / 73卷 / 04期

基金：

英国医学研究理事会;

关键词：

D O I：

10.1016/0030-4220(92)90325-K

中图分类号：

R78 [口腔科学];

学科分类号：

1003 ;

摘要：

A case is described of a boy with dentinogenesis imperfecta associated with osteogenesis imperfecta. The dentin of extracted deciduous teeth was found to show an abrupt transition to a normal tubular structure before a reversion to the more typical structure seen in dentinogenesis imperfecta. This change in the dentin appeared to have occurred in a chronologic manner. The possibilities that either a metabolic disturbance or a temporary reduced expression of the mutant gene had caused the abnormality and could account for the unusual histologic findings are discussed.

引用

页码：461 / 464

页数：4