Preimplantation genetic diagnosis for spinal and bulbar muscular atrophy (SBMA)

被引:0
|
作者
Ioannis Georgiou
Karen Sermon
Willy Lissens
Anick De Vos
Peter Platteau
Dimitrios Lolis
Andre Van Steirteghem
Inge Liebaers
机构
[1] Genetics and IVF Unit,
[2] Department of Obstetrics and Gynecology,undefined
[3] Medical School,undefined
[4] University of Ioannina,undefined
[5] 45500 Ioannina,undefined
[6] Greece,undefined
[7] Centre for Medical Genetics,undefined
[8] University Hospital,undefined
[9] Dutch-Speaking Brussels Free University,undefined
[10] Laarbeeklaan 101,undefined
[11] 1090 Brussels,undefined
[12] Belgium,undefined
[13] Centre for Reproductive Medicine,undefined
[14] University Hospital,undefined
[15] Dutch-Speaking Brussels Free University,undefined
[16] Laarbeeklaan 101,undefined
[17] 1090 Brussels,undefined
[18] Belgium,undefined
来源
Human Genetics | 2001年 / 108卷
关键词
Androgen Receptor; Preimplantation Genetic Diagnosis; Intracytoplasmic Sperm Injection; Carrier Female; Androgen Receptor Gene;
D O I
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中图分类号
学科分类号
摘要
X-linked spinal and bulbar muscular atrophy is characterized by adult onset motor neuron disease and results from a defect in the androgen receptor. The disease is caused by a dynamic mutation in the first exon of the androgen receptor gene, involving a CAG trinucleotide repeat. We have developed a single-cell polymerase chain reaction assay for the androgen receptor gene and describe the application of this assay for preimlantation genetic diagnosis (PGD) in a couple at risk, where the female partner is a carrier of 47 repeats. Diagnosis was based on the detection of both normal and expanded alleles. Allele dropout of the expanded allele was observed in only 1 of 25 lymphoblasts of the carrier and of a non-expanded allele in 1 of 20 research blastomeres tested before the actual PGD. One contraction of four repeats was also found in the carrier's lymphoblasts. Neither expansions nor contractions were observed in the blastomeres biopsied from 11 embryos. Two embryos were unaffected, eight were female carriers and one was an affected male embryo.
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页码:494 / 498
页数:4
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