Renal transplantations from parents to siblings with autosomal recessive Alport syndrome caused by a rearrangement in an intronic antisense Alu element in the COL4A3 gene led to different outcomes

被引:0
作者
Jun-ya Kaimori
Naotsugu Ichimaru
Yoshitaka Isaka
Fusako Hashimoto
Xuejun Fu
Yuya Hashimura
Hiroshi Kaito
Kazumoto Iijima
Masahiro Kyo
Tomoko Namba
Yoshitsugu Obi
Masaki Hatanaka
Isao Matsui
Yoshitsugu Takabatake
Masayoshi Okumi
Koji Yazawa
Norio Nonomura
Hiromi Rakugi
Shiro Takahara
机构
[1] Osaka University Graduate School of Medicine,Department of Advanced Technology for Transplantation
[2] Kobe University Graduate School of Medicine,Department of Pediatrics
[3] Sakurabashi Iseikai Clinic,Department of Specific Organ Regulation (Urology)
[4] Osaka University Graduate School of Medicine,Department of Geriatrics and Nephrology
[5] Osaka University Graduate School of Medicine,undefined
关键词
Alport syndrome; Anti-GBM nephritis; Cryptic exon; Renal transplantation;
D O I
10.1007/s13730-012-0049-7
中图分类号
学科分类号
摘要
Two siblings with autosomal recessive Alport syndrome (ARAS) obtained renal transplants from their consanguineous parents. Their COL4A3 mRNA transcripts were disrupted by a 139 bp intronic sequence between exon 48 and 49, which was derived from an antisense Alu element in this intron. The new amino acid sequence from the cryptic exon was terminated by a stop codon at the 1511th codon, resulting in the loss of 76 % α3(IV)NC1. This is the first case report of kidney transplantations between ARAS-homozygous siblings and their heterozygous parents. The brother experienced acute rejection just after transplantation and post-transplantation anti-glomerular basement membrane (GBM) nephritis, whereas the sister has experienced no problems to date. The anti-GBM nephritis could have resulted from the acute rejection. The COL4A3 gene heterozygous mutated parents, who are possibly at risk for thin basement membrane disease, have maintained their renal functions without urinary abnormalities after renal transplantation to date.
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页码:98 / 101
页数:3
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