Eradication of advanced pelvic hydatid bone disease after limb salvage surgery - 5-Year follow-up: A case report

被引:8
作者
Khan M.S. [1 ]
Hashmi P.M. [2 ]
Khan D. [3 ]
机构
[1] Department of Orthopaedics, Shah Bhitai District Government Hospital, Hyderabad
[2] Head Section of Orthopaedics, Department of Surgery, Aga Khan University Hospital, Karachi
[3] Department of Radiology, Aga Khan University Hospital, Karachi
关键词
Hydatid bone disease; Limb salvage surgery;
D O I
10.1186/1752-1947-9-21
中图分类号
学科分类号
摘要
Introduction: Echinococcosis is produced by the larval stage of Echinococcus granulosus; it is a parasitic disease which is seen rarely in humans and has adverse outcomes. We report a case of advanced pelvic hydatid bone disease with successful limb salvage surgery. Our patient had a 5-year follow-up without recurrence which is a rarity as per the literature. Early diagnosis and prompt medical therapy are necessary for effective management whereas delayed diagnosis is always fraught with the risk of recurrence and sepsis. Case presentation: In 2009, a 30-year-old woman, native of Karachi (Sindhi ethnicity), presented at our clinic with history of a pathological fracture 11 years earlier. Her fracture was initially misdiagnosed and fixed. Subsequently she had persistent disease that progressed with time. Following this she underwent multiple surgeries and the diagnosis of hydatid disease was made but despite multiple debridements and medical therapy she was not cured and finally she was offered a hemipelvectomy (limb sacrifice). On presentation to our hospital she was counseled regarding options of hemipelvectomy versus a limb salvage form of modified internal hemipelvectomy and wide margin resection. She opted for limb salvage. She underwent internal hemipelvectomy with wide margin resection of soft tissue and proximal femur along with postoperative albendazole therapy. She was able to walk again after a very long period. Currently she is 5-years postreconstructive surgery. She is infection free and ambulant without support. Conclusions: Hydatid bone disease is a rare entity in our part of the world but a careful history and thorough look at the initial images of our patient would have led to the suspicion of pathologic fracture and subsequent early diagnosis of this difficult problem. A second important learning point in this case was the lack of early referral to a center where this difficult problem could have been handled effectively. This could have minimized the physical, mental and financial stress to the patient and her family. © 2015 Khan et al.; licensee BioMed Central.
引用
收藏
相关论文
共 20 条
[1]  
Agarwal S., Shah A., Kadhi S.K., Rooney R.J., Hydatid bone disease of the pelvis. A report of two cases and review of the literature, Clin Orthop Relat Res, 280, pp. 251-255, (1992)
[2]  
Szypryt E.P., Morris D.L., Mulholland R.C., Combined chemotherapy and surgery for hydatid bone disease, J Bone Joint Surg (Br), 69, 1, pp. 141-144, (1987)
[3]  
Uzel M., Hiz M., Aydingoz O., Curettage, local heat and cement application in echinococcosis of bone, Joint Meeting of EMSOS-AMSTS: Florence, Italy
[4]  
1995, (1995)
[5]  
El Ibrahimi A., Ankouz A., Daoudi A., Elmrini A., Pelvic bone and hip joint hydatid disease revealing a retroperitoneal location, Orthop Rev (Pavia), 1, 1, (2009)
[6]  
Porat S., Joseph K.N., Hydatid disease of bone: A case report and review of the literature, Isr J Med Sci, 14, 2, pp. 223-227, (1978)
[7]  
Sapkas G.S., Stathakopoulos D.P., Babis G.C., Tsarouchas J.K., Hydatid disease of bones and joints: 8 Cases followed for 4-16 years, Acta Orthop, 69, 1, pp. 89-94, (1998)
[8]  
Mnaymneh W., Yacoubian V., Bikhazi K., Hydatidosis of the pelvic girdle: Treatment by partial pelvectomy, J Bone Joint Surg Am, 59, pp. 538-540, (1977)
[9]  
Natarajan M.V., Kumar A.K., Sivaseelam A., Iyakutty P., Raja M., Rajagopal T.S., Using a custom megaprosthesis to treat hydatidosis of bone: A report of 3 cases, J Orthop Surg-Hong Kong, 10, 2, pp. 203-205, (2002)
[10]  
Zlitni M., Ezzaouia K., Lebib H., Karray M., Kooli M., Mestiri M., Hydatid cyst of bone: Diagnosis and treatment, World J Surg, 25, 1, pp. 75-82, (2001)