Early Detection and Management of Prader-Willi Syndrome in Egyptian Patients

被引:4
|
作者
El-Bassyouni, Hala T. [1 ]
Hassan, Nagwa [2 ]
Mahfouz, Inas [2 ]
Abd-Elnaby, Azza E. [3 ]
Mostafa, Mostafa, I [4 ]
Tosson, Angie M. S. [5 ]
机构
[1] Natl Res Ctr, Dept Clin Genet, El Tahreer St, Cairo 12622, Egypt
[2] Natl Res Ctr, Dept Nutr, Cairo, Egypt
[3] Natl Res Ctr, Dept Human Cytogenet, Cairo, Egypt
[4] Natl Res Ctr, Dept Orodent Genet, Cairo, Egypt
[5] Cairo Univ, Fac Med, Dept Pediat, Cairo, Egypt
关键词
early PWS detection; management; oro-dental findings; PWS diagnostic strategy; weight loss; OBESITY; DELETION; ANKYLOGLOSSIA; PREVALENCE; GENETICS; BEHAVIOR;
D O I
10.1055/s-0039-1695042
中图分类号
R72 [儿科学];
学科分类号
100202 ;
摘要
Prader-Willi syndrome (PWS) is a distinct neurodevelopmental disorder associated with the deletion within the chromosomal 15q11-q13 region or uniparental disomy of chromosome 15. The etiologic heterogeneity of PWS makes it very difficult to establish uniform diagnostic methods which would result in the detection of most affected individuals. The objective was to report the clinical criteria and oro-dental features in PWS, to report the effect of diet and laser acupuncture on PWS and highlighted an easy effective method for early diagnosis of individuals with PWS. The study included seventeen cytogenetically proven individuals with Prader-Willi syndrome. These patients were subjected to meticulous history taking, clinical examination including oro-dental examination, bone densitometry and neuropsychiatric evaluation. They received laser acupuncture sessions in addition to nutrition intervention. All cases had characteristic facies, hypotonia and various psychosocial difficulties. Other criteria of PWS were present in different percentages. Karyotyping revealed deletion 15q11-q13 in 6 patients, and fluorescence in situ hybridization (FISH) revealed a microdeletion in 15q11-q13 in the other 11 patients. To our knowledge, partial ankyloglossia, median grooved tongue and hypodontia have not previously been reported in PWS patients. Laser acupuncture sessions and diet were effective in weight decline for PWS patients. Our study emphasizes the importance of early detection of PWS, laser sessions, diet restriction and oro-dental examination in the follow up of patients with Prader Willi syndrome.
引用
收藏
页码:179 / 186
页数:8
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