Chylotamponade: An unusual presentation of Gorham's syndrome

被引:15
|
作者
Swelstad, MR [1 ]
Frumiento, C [1 ]
Garry-McCoy, A [1 ]
Agni, R [1 ]
Weigel, TL [1 ]
机构
[1] Univ Wisconsin, Ctr Med, Dept Surg, Madison, WI 53792 USA
来源
ANNALS OF THORACIC SURGERY | 2003年 / 75卷 / 05期
关键词
D O I
10.1016/S0003-4975(02)04776-8
中图分类号
R5 [内科学];
学科分类号
1002 ; 100201 ;
摘要
Gorham's Syndrome, also known as massive osteolysis or "vanishing bone disease" results from lymphangiomatosis with adjacent bone resorption. Chylothorax is a common complication in cases of mediastinal involvement. We report a case of Gorham's Syndrome presenting as chylotamponade successfully treated with pericardial drainage, early parenteral nutritional support, bilateral pleurodesis for chylous effusions, and adjuvant external beam radiation. (C) 2003 by The Society of Thoracic Surgeons.
引用
收藏
页码:1650 / 1652
页数:3
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