Chylotamponade: An unusual presentation of Gorham's syndrome

被引：16

作者：

Swelstad, MR ^{[1
]}

Frumiento, C ^{[1
]}

Garry-McCoy, A ^{[1
]}

Agni, R ^{[1
]}

Weigel, TL ^{[1
]}

机构：

[1] Univ Wisconsin, Ctr Med, Dept Surg, Madison, WI 53792 USA

来源：

ANNALS OF THORACIC SURGERY | 2003年 / 75卷 / 05期

关键词：

D O I：

10.1016/S0003-4975(02)04776-8

中图分类号：

R5 [内科学];

学科分类号：

1002 ; 100201 ;

摘要：

Gorham's Syndrome, also known as massive osteolysis or "vanishing bone disease" results from lymphangiomatosis with adjacent bone resorption. Chylothorax is a common complication in cases of mediastinal involvement. We report a case of Gorham's Syndrome presenting as chylotamponade successfully treated with pericardial drainage, early parenteral nutritional support, bilateral pleurodesis for chylous effusions, and adjuvant external beam radiation. (C) 2003 by The Society of Thoracic Surgeons.

引用

页码：1650 / 1652

页数：3

共 6 条

[1] GORHAM MASSIVE OSTEOLYSIS - THE ROLE OF RADIATION-THERAPY AND A REVIEW OF THE LITERATURE [J].

DUNBAR, SF ;

ROSENBERG, A ;

MANKIN, H ;

ROSENTHAL, D ;

SUIT, HD .

INTERNATIONAL JOURNAL OF RADIATION ONCOLOGY BIOLOGY PHYSICS, 1993, 26 (03) :491-497

[2] CHYLOPERICARDIUM WITH MULTIPLE LYMPHANGIOMA OF BONE [J].

GOLDSTEIN, MR ;

BENCHIMOL, A ;

CORNELL, W ;

LONG, DR .

NEW ENGLAND JOURNAL OF MEDICINE, 1969, 280 (19) :1034-+

[3] RADIOTHERAPY OF MORBUS GORHAM-STOUT - THE BIOLOGICAL VALUE OF LOW IRRADIATION DOSE [J].

HANDLZELLER, L ;

HOHENBERG, G .

BRITISH JOURNAL OF RADIOLOGY, 1990, 63 (747) :206-208

[4] MASSIVE OSTEOLYSIS COMPLICATED BY CHYLOTHORAX SUCCESSFULLY TREATED BY PLEURODESIS [J].

PATRICK, JH .

JOURNAL OF BONE AND JOINT SURGERY-BRITISH VOLUME, 1976, 58 (03) :347-349

[5] GORHAM SYNDROME [J].

PEDICELLI, G ;

MATTIA, P ;

ZORZOLI, AA ;

SORRONE, A ;

DEMARTINO, F ;

SCIOTTO, V .

JAMA-JOURNAL OF THE AMERICAN MEDICAL ASSOCIATION, 1984, 252 (11) :1449-1451

[6] CHYLOTHORAX IN GORHAMS SYNDROME - A COMMON COMPLICATION OF A RARE DISEASE [J].

TIE, MLH ;

POLAND, GA ;

ROSENOW, EC .

CHEST, 1994, 105 (01) :208-213

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