The prevalence of the FMR1 and FMR2 mutations among preschool children with language delay

被引:22
作者
Mazzocco, MMM
Myers, GF
Hamner, JL
Panoscha, R
Shapiro, BK
Reiss, AL
机构
[1] Kennedy Krieger Inst, Behav Neurogenet Res Ctr, Baltimore, MD 21205 USA
[2] Kennedy Krieger Inst, Ctr Learning & Disorders, Baltimore, MD 21205 USA
[3] Johns Hopkins Univ, Sch Med, Dept Psychiat, Baltimore, MD 21205 USA
[4] Johns Hopkins Univ, Sch Med, Dept Pediat, Baltimore, MD 21205 USA
[5] Johns Hopkins Univ, Sch Med, Dept Neurol, Baltimore, MD 21205 USA
关键词
D O I
10.1016/S0022-3476(98)70306-3
中图分类号
R72 [儿科学];
学科分类号
100202 ;
摘要
We examined the prevalence of the fragile X mental retardation (FMR1) full mutation and fragile X E mutation (FMR2) among preschoolers evaluated for language delay. A total of 534 preschoolers recruited from a Developmental Pediatric or Speech and Language Disorders clinic were tested with Southern blot and polymerase chain reaction DNA analyses; 3 were found to have the FMR1 full mutation. None of the 534 children tested positive for the FMR2 full mutation; however, 3 children had unusually small FMR2 alleles suggestive of FMR2 deletions. Screening for fragile X among language-delayed preschoolers is warranted, particularly when there is a family history of mental retardation, but regardless of sex or the presence of behavioral or physical features associated with the fragile X phenotype. The potential benefit of screening for FMR2 alterations is an unexpected implication of the study and is worthy of continued exploration.
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收藏
页码:795 / 801
页数:7
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