Siblings of children with Williams syndrome: Correlates of psychosocial adjustment and sibling relationship quality

被引:15
作者
Cebula, Katie [1 ]
Gillooly, Amanda [1 ]
Coulthard, Laura K. [2 ]
Riby, Deborah M. [2 ]
Hastings, Richard P. [3 ,4 ]
机构
[1] Univ Edinburgh, Moray House Sch Educ & Sport, Edinburgh, Midlothian, Scotland
[2] Univ Durham, Dept Psychol, Durham, England
[3] Univ Warwick, Ctr Educ Dev Appraisal & Res, Coventry, W Midlands, England
[4] Monash Univ, Ctr Dev Psychiat & Psychol, Dept Psychiat, Sch Clin Sci,Monash Hlth, Melbourne, Vic, Australia
关键词
Family; Sibling; Williams syndrome; AUTISM SPECTRUM DISORDER; BEHAVIORAL PHENOTYPES; YOUNG-CHILDREN; DIFFICULTIES QUESTIONNAIRE; INTELLECTUAL DISABILITY; PSYCHOMETRIC PROPERTIES; ANXIETY SYMPTOMS; SOCIAL PHENOTYPE; PRADER-WILLI; FRAGILE-X;
D O I
10.1016/j.ridd.2019.103496
中图分类号
G76 [特殊教育];
学科分类号
040109 ;
摘要
Background: Previous research has examined adjustment in parents of children with Williams syndrome (WS), but little is known about sibling outcomes. Aims: To explore sibling adjustment and relationship quality, and their demographic, psychological and behavioural phenotypic correlates from the perspective of caregivers and siblings in families of children with WS. Methods and procedures: Forty-one caregivers of children with WS participated in this questionnaire study on the adjustment and relationship quality of the siblings. In 31 of these families, self-report data were also provided by the siblings themselves. Data were also gathered on potential correlates, including anxiety and social functioning in the child with WS, caregiver mental health, and sibling social support. Outcomes and results: Sibling adjustment was similar to population norms, though significantly increased caregiver-reported emotional difficulties were found. Siblings reported greater behavioural, emotional and relationship difficulties than caregivers perceived them to have. Some significant associations were found between the behaviour of the child with WS, sibling behaviour problems and sibling relationship quality. Conclusions and implications: A picture of relatively positive sibling adjustment and relationships emerged, but findings of individual differences and some emotional difficulties emphasise the need for an individualised approach to support in families of children with WS.
引用
收藏
页数:12
相关论文
共 76 条
[1]   CHILD ADOLESCENT BEHAVIORAL AND EMOTIONAL-PROBLEMS - IMPLICATIONS OF CROSS-INFORMANT CORRELATIONS FOR SITUATIONAL SPECIFICITY [J].
ACHENBACH, TM ;
MCCONAUGHY, SH ;
HOWELL, CT .
PSYCHOLOGICAL BULLETIN, 1987, 101 (02) :213-232
[2]   Comparing parental stress of children with neurodevelopmental disorders: The case of Williams syndrome, Down syndrome and autism spectrum disorders [J].
Ashworth, Maria ;
Palikara, Olympia ;
Van Herwegen, Jo .
JOURNAL OF APPLIED RESEARCH IN INTELLECTUAL DISABILITIES, 2019, 32 (05) :1047-1057
[3]   The neurocognitive profile of Williams syndrome: A complex pattern of strengths and weaknesses [J].
Bellugi, U ;
Lichtenberger, L ;
Jones, W ;
Lai, Z ;
St George, M .
JOURNAL OF COGNITIVE NEUROSCIENCE, 2000, 12 :7-29
[4]   Adaptive functioning in Williams syndrome and its relation to demographic variables and family environment [J].
Brawn, Gabrielle ;
Porter, Melanie .
RESEARCH IN DEVELOPMENTAL DISABILITIES, 2014, 35 (12) :3606-3623
[5]  
Bronfenbrenner U., 2005, MAKING HUMAN BEINGS
[6]  
Bronfenbrenner W., 1979, The ecology of human development: Experiments by nature and design
[7]  
BUHRMESTER D, 1990, CHILD DEV, V61, P1387, DOI 10.2307/1130750
[8]   Applied Behavior Analysis Programs for Autism: Sibling Psychosocial Adjustment During and Following Intervention Use [J].
Cebula, Katie R. .
JOURNAL OF AUTISM AND DEVELOPMENTAL DISORDERS, 2012, 42 (05) :847-862
[9]   Psychological Well-Being of Mothers and Siblings in Families of Girls and Women with Rett Syndrome [J].
Cianfaglione, Rina ;
Hastings, Richard P. ;
Felce, David ;
Clarke, Angus ;
Kerr, Michael P. .
JOURNAL OF AUTISM AND DEVELOPMENTAL DISORDERS, 2015, 45 (09) :2939-2946
[10]  
Constantino J. N., 2012, SOCIAL RESPONSIVENES