Primary Sclerosing Cholangitis Complicated with Aphthoid Colitis Difficult to Diagnose from IgG4-Related Sclerosing Cholangitis

被引：0
作者：
Imai, Jin [1 ,2 ]
Ichikawa, Hitoshi [2 ,3 ]
Kaneko, Motoki [1 ,2 ]
Ito, Hiroyuki [2 ]
Takashimizu, Shinji [2 ]
Shirai, Takayuki [2 ]
Tajiri, Takuma [4 ]
Watanabe, Norihito [2 ]
Suzuki, Hidekazu [1 ]
机构：
[1] Tokai Univ, Dept Gastroenterol, Sch Med, Isehara, Kanagawa, Japan
[2] Tokai Univ, Dept Gastroenterol, Sch Med, Hachioji Hosp, Tokyo, Japan
[3] Keio Univ, Ctr Prevent Med, Sch Med, Tokyo, Japan
[4] Tokai Univ, Dept Pathol, Hachioji Hosp, Sch Med, Tokyo, Japan
来源：
CASE REPORTS IN GASTROENTEROLOGY | 2022年 / 16卷 / 01期
基金：
日本学术振兴会;
关键词：
Primary sclerosing cholangitis; Aphtoid colitis; IgG4-related sclerosing cholangitis; IMMUNOGLOBULIN G4-ASSOCIATED CHOLANGITIS; AUTOIMMUNE PANCREATITIS; DISEASE;
D O I：
10.1159/000521538
中图分类号：
R57 [消化系及腹部疾病];
学科分类号：
摘要：
A 19-year-old man visited our hospital because of diarrhea and blood and liver dysfunction. Magnetic and endoscopic retrograde cholangiography revealed diffuse narrowing of the common biliary tract and intrahepatic biliary tract. A biopsy specimen from the narrowed area of the common biliary tract revealed IgG4-related sclerosing cholangitis (IgG4-SC). Colonoscopy showed multiple aphthoid colitis. He was treated with corticosteroids, and the levels of hepatobiliary enzymes, IgG, and IgG4 gradually decreased. This is an extremely rare case of colitis in which the patient had a phenotype of sclerosing cholangitis similar to IgG4-SC, which was finally diagnosed as primary sclerosing cholangitis.
引用
收藏
页码：23 / 28
页数：6
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