Bilateral panuveitis in a child with hypohidrotic ectodermal dysplasia

被引:4
作者
Rodriguez, N
Eliott, D
Garcia-Valenzuela, E
Baker, J
机构
[1] Wayne State Univ, Kresge Eye Inst, Sch Med, Detroit, MI 48201 USA
[2] Wayne State Univ, Childrens Hosp Michigan, Sch Med, Detroit, MI 48201 USA
关键词
D O I
10.1016/S0002-9394(02)01570-2
中图分类号
R77 [眼科学];
学科分类号
100212 ;
摘要
PURPOSE: To report a case of bilateral panuveitis in a patient with hypohidrotic ectodermal dysplasia. DESIGN: Interventional case report. METHODS: A 6,year,old African,American boy with hypohidrotic ectodermal dysplasia presented with pain, photophobia, and decreased vision in both eyes. RESULTS: Findings included severe bilateral panuveitis with optic disk edema, macular epiretinal membrane, peripheral retinal vasculitis, and retinitis. All other known causes of panuveitis were explored and ruled out. CONCLUSIONS: The abnormal development of tissues of ectodermal origin evident in hypohidrotic ectodermal dysplasia may include a predisposition to panuveitis. (C) 2002 by Elsevier Science Inc. All rights reserved.
引用
收藏
页码:443 / 445
页数:3
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