Expanded Newborn Screening for Inborn Errors of Metabolism and Genetic Characteristics in a Chinese Population

被引:6
|
作者
Guo, Kejian [1 ]
Zhou, Xuan [2 ,3 ]
Chen, Xigui [1 ]
Wu, Yili [2 ,3 ,4 ]
Liu, Chuanxin [2 ,4 ]
Kong, Qingsheng [4 ,5 ]
机构
[1] Jining Maternal & Child Hlth Care Hosp, Jining, Peoples R China
[2] Jining Med Univ, Dept Psychiat, Jining, Peoples R China
[3] Jining Med Univ, Shandong Key Lab Behav Med, Jining, Peoples R China
[4] Jining Med Univ, Collaborat Innovat Ctr Birth Defect Res & Transfo, Jining, Peoples R China
[5] Jining Med Univ, Dept Biochem, Jining, Peoples R China
来源
FRONTIERS IN GENETICS | 2018年 / 9卷
基金
中国国家自然科学基金;
关键词
newborn screening; inborn errors of metabolism; incidence of IEMs; IEMs-associated gene mutation; TANDEM MASS-SPECTROMETRY; METHYLMALONIC ACIDEMIA; CARNITINE DEFICIENCY; MAINLAND CHINA; DISORDERS; MUTATIONS; PILOT; PHENYLKETONURIA; PROVINCE; PROGRAM;
D O I
10.3389/fgene.2018.00122
中图分类号
Q3 [遗传学];
学科分类号
071007 ; 090102 ;
摘要
The incidence of inborn errors of metabolisms (IEMs) varies dramatically in different countries and regions. Expanded newborn screening for IEMs by tandem mass spectrometry (MS/MS) is an efficient approach for early diagnosis and presymptomatic treatment to prevent severe permanent sequelae and death. To determine the characteristics of IEMs and IEMs-associated mutations in newborns in Jining area, China, 48,297 healthy neonates were recruited for expanded newborn screening by MS/MS. The incidence of IEMs was 1/1178 in Jining, while methylmalonic acidemia, phenylketonuria, and primary carnitine deficiency ranked the top 3 of all detected IEMs. Thirty mutations in nine IEMs-associated genes were identified in 28 confirmed cases. As 19 cases with the mutations in phenylalanine hydroxylase (PAH), solute carrier family 22 member 5 (SLC22A5), and methylmalonic aciduria (cobalamin deficiency) cblC type with homocystinuria (MMACHC) genes, respectively, it suggested that mutations in the PAH, SLC22A5, and MMACHC genes are the predominant causes of IEMs, leading to the high incidence of phenylketonuria, primary carnitine deficiency, and methylmalonic acidemia, respectively. Our work indicated that the overall incidence of IEMs is high and the mutations in PAH, SLC22A5, and MMACHC genes are the leading causes of IEMs in Jining area. Therefore, it is critical to increase the coverage of expanded newborn screening by MS/MS and prenatal genetic consulting in Jining area.
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页数:7
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