Old and new tools in the clinical diagnosis of inherited bone marrow failure syndromes

被引:24
作者
West, Allison H. [1 ]
Churpek, Jane E. [1 ,2 ]
机构
[1] Univ Chicago, Comprehens Canc Ctr, Sect Hematol Oncol, Chicago, IL 60637 USA
[2] Univ Chicago, Ctr Clin Canc Genet, Chicago, IL 60637 USA
基金
美国国家卫生研究院;
关键词
SEVERE CONGENITAL NEUTROPENIA; SHWACHMAN-DIAMOND SYNDROME; FANCONI-ANEMIA; MYELODYSPLASTIC SYNDROME; SOMATIC MOSAICISM; GATA2; MUTATIONS; TELOMERE LENGTH; BLACKFAN ANEMIA; APLASTIC-ANEMIA; PATHOPHYSIOLOGY;
D O I
10.1182/asheducation-2017.1.79
中图分类号
G40 [教育学];
学科分类号
040101 ; 120403 ;
摘要
Patients with inherited bone marrow failure syndromes (IBMFSs) classically present with specific patterns of cytopenias along with congenital anomalies and/or other physical features that are often recognizable early in life. However, increasing application of genomic sequencing and clinical awareness of subtle disease presentations have led to the recognition of IBMFS in pediatric and adult populations more frequently than previously realized, such as those with early onset myelodysplastic syndrome (MDS). Given the well-defined differences in clinical management needs and outcomes for aplastic anemia, acute myeloid leukemia, and MDS in patients with an IBMFS vs those occurring sporadically, as well as nonhematologic comorbidities in patients with IBMFSs, it is critical for hematologists to understand how to approach screening for the currently known IBMFSs. This review presents a practical approach for the clinical hematologist that outlines when to suspect an IBMFS and how to use various diagnostic tools, from physical examination to screening laboratory tests and genomics, for the diagnosis of the most frequent IBMFSs: Fanconi anemia, telomere biology disorders, Diamond-Blackfan anemia, GATA2 deficiency syndrome, Shwachman-Diamond syndrome, and severe congenital neutropenia.
引用
收藏
页码:79 / 87
页数:9
相关论文
共 53 条
[1]   Compound inheritance of a low-frequency regulatory SNP and a rare null mutation in exon-junction complex subunit RBM8A causes TAR syndrome [J].
Albers, Cornelis A. ;
Paul, Dirk S. ;
Schulze, Harald ;
Freson, Kathleen ;
Stephens, Jonathan C. ;
Smethurst, Peter A. ;
Jolley, Jennifer D. ;
Cvejic, Ana ;
Kostadima, Myrto ;
Bertone, Paul ;
Breuning, Martijn H. ;
Debili, Najet ;
Deloukas, Panos ;
Favier, Remi ;
Fiedler, Janine ;
Hobbs, Catherine M. ;
Huang, Ni ;
Hurles, Matthew E. ;
Kiddle, Graham ;
Krapels, Ingrid ;
Nurden, Paquita ;
Ruivenkamp, Claudia A. L. ;
Sambrook, Jennifer G. ;
Smith, Kenneth ;
Stemple, Derek L. ;
Strauss, Gabriele ;
Thys, Chantal ;
van Geet, Chris ;
Newbury-Ecob, Ruth ;
Ouwehand, Willem H. ;
Ghevaert, Cedric .
NATURE GENETICS, 2012, 44 (04) :435-U248
[2]   Telomere length in inherited bone marrow failure syndromes [J].
Alter, Blanche P. ;
Giri, Neelam ;
Savage, Sharon A. ;
Rosenberg, Philip S. .
HAEMATOLOGICA, 2015, 100 (01) :49-54
[3]   Telomere length is associated with disease severity and declines with age in dyskeratosis congenita [J].
Alter, Blanche P. ;
Rosenberg, Philip S. ;
Giri, Neelam ;
Baerlocher, Gabriela M. ;
Lansdorp, Peter M. ;
Savage, Sharon A. .
HAEMATOLOGICA-THE HEMATOLOGY JOURNAL, 2012, 97 (03) :353-359
[4]   Malignancies and survival patterns in the National Cancer Institute inherited bone marrow failure syndromes cohort study [J].
Alter, Blanche P. ;
Giri, Neelam ;
Savage, Sharon A. ;
Peters, June A. ;
Loud, Jennifer T. ;
Leathwood, Lisa ;
Carr, Ann G. ;
Greene, Mark H. ;
Rosenberg, Philip S. .
BRITISH JOURNAL OF HAEMATOLOGY, 2010, 150 (02) :179-188
[5]  
[Anonymous], 1993, GENEREVIEWS
[6]   The telomere syndromes [J].
Armanios, Mary ;
Blackburn, Elizabeth H. .
NATURE REVIEWS GENETICS, 2012, 13 (10) :693-704
[7]   Telomerase mutations in families with idiopathic pulmonary fibrosis [J].
Armanios, Mary Y. ;
Chen, Julian J. -L. ;
Cogan, Joy D. ;
Alder, Jonathan K. ;
Ingersoll, Roxann G. ;
Markin, Cheryl ;
Lawson, William E. ;
Xie, Mingyi ;
Vulto, Irma ;
Phillips, John A., III ;
Lansdorp, Peter M. ;
Greider, Carol W. ;
Loyd, James E. .
NEW ENGLAND JOURNAL OF MEDICINE, 2007, 356 (13) :1317-1326
[8]   Flow cytometry and FISH to measure the average length of telomeres (flow FISH) [J].
Baerlocher, Gabriela M. ;
Vulto, Irma ;
de Jong, Gary ;
Lansdorp, Peter M. .
NATURE PROTOCOLS, 2006, 1 (05) :2365-2376
[9]   Genetics and Pathophysiology of Severe Congenital Neutropenia Syndromes Unrelated to Neutrophil Elastase [J].
Boztug, Kaan ;
Klein, Christoph .
HEMATOLOGY-ONCOLOGY CLINICS OF NORTH AMERICA, 2013, 27 (01) :43-+
[10]   Ataxia-Pancytopenia Syndrome Is Caused by Missense Mutations in SAMD9L [J].
Chen, Dong-Hui ;
Below, Jennifer E. ;
Shimamura, Akiko ;
Keel, Sioban B. ;
Matsushita, Mark ;
Wolff, John ;
Sul, Youngmee ;
Bonkowski, Emily ;
Castella, Maria ;
Taniguchi, Toshiyasu ;
Nickerson, Deborah ;
Papayannopoulou, Thalia ;
Bird, Thomas D. ;
Raskind, Wendy H. .
AMERICAN JOURNAL OF HUMAN GENETICS, 2016, 98 (06) :1146-1158