Standard screening methods underreport AAV-mediated transduction and gene editing

被引:50
作者
Lang, Jonathan F. [1 ,2 ]
Toulmin, Sushila A. [1 ,2 ]
Brida, Kasey L. [1 ]
Eisenlohr, Laurence C. [1 ,2 ]
Davidson, Beverly L. [1 ,2 ]
机构
[1] Childrens Hosp Philadelphia, Philadelphia, PA 19104 USA
[2] Univ Penn, Perelman Sch Med, Dept Pathol & Lab Med, Philadelphia, PA 19104 USA
关键词
IN-VIVO; TRANSFER SUPERIOR; EXPRESSION; VECTORS; MOUSE; DELIVERY; THERAPY; TROPISM; MICE; STEM;
D O I
10.1038/s41467-019-11321-7
中图分类号
O [数理科学和化学]; P [天文学、地球科学]; Q [生物科学]; N [自然科学总论];
学科分类号
07 ; 0710 ; 09 ;
摘要
Conventional methods to discern adeno-associated virus (AAV) vector transduction patterns are based on high, stable expression of a reporter gene. As a consequence, conventionally described tropisms omit cell types that undergo transient transduction, or have low but undetectable levels of reporter expression. This creates a blind spot for AAV-based genome editing applications because only minimal transgene expression is required for activity. Here, we use editing-reporter mice to fill this void. Our approach sensitively captures both high and low transgene expression from AAV vectors. Using AAV8 and other serotypes, we demonstrate the superiority of the approach in a side-by-side comparison with traditional methods, demonstrate numerous, previously unknown sites of AAV targeting, and better predict the gene editing footprint after AAV-CRISPR delivery. We anticipate that this system, which captures the full spectrum of transduction patterns from AAV vectors in vivo, will be foundational to current and emerging AAV technologies.
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页数:10
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