Fetal surgery for myelomeningocele is effective: a critical look at the whys

被引:43
作者
Meuli, Martin [1 ,2 ]
Moehrlen, Ueli [1 ,2 ]
机构
[1] Univ Childrens Hosp Zurich, Dept Pediat Surg, CH-8032 Zurich, Switzerland
[2] Univ Zurich, Zurich Ctr Fetal Diag & Therapy, Zurich, Switzerland
关键词
Fetal surgery; Myelomeningocele; Spina bifida; Prenatal diagnosis; IN-UTERO REPAIR; TISSUE ENGINEERING APPROACH; SPINAL-CORD LESION; HINDBRAIN HERNIATION; NEUROLOGICAL FUNCTION; ENDOSCOPIC COVERAGE; PRENATAL CLOSURE; SMOOTH-MUSCLE; HUMAN FETUSES; FOLLOW-UP;
D O I
10.1007/s00383-014-3524-8
中图分类号
R72 [儿科学];
学科分类号
100202 ;
摘要
Formerly, the disastrous cluster of neurologic deficits and associated neurogenic problems in patients with myelomeningocele (MMC) was generally thought to solely result from the primary malformation, i.e., failure of neurulation. Today, however, there is no doubt that a dimensional additional pathogenic mechanism exists. Most likely, it contributes much more to loss of neurologic function than non-neurulation does. Today, there is a large body of compelling experimental and clinical evidence confirming that the exposed part of the non-neurulated spinal cord is progressively destroyed during gestation, particularly so in the third trimester. These considerations gave rise to the two-hit-pathogenesis of MMC with non-neurulation being the first and consecutive in utero acquired neural tissue destruction being the second hit. This novel pathophysiologic understanding has obviously triggered the question whether the serious and irreversible functional loss caused by the second hit could not be prevented or, at least, significantly alleviated by timely protecting the exposed spinal cord segments, i.e., by early in utero repair of the MMC lesion. Based on this intriguing hypothesis and the above-mentioned data, human fetal surgery for MMC was born in the late nineties of the last century and has made its way to become a novel standard of care, particularly after the so-called "MOMS Trial". This trial, published in the New England Journal of Medicine, has indisputably shown that overall, open prenatal repair is distinctly better than postnatal care alone. Finally, a number of important other topics deserve being mentioned, including the necessity to work on the up till now immature endoscopic fetal repair technique and the need for concentration of these extremely challenging cases to a small number of really qualified fetal surgery centers worldwide. In conclusion, despite the fact that in utero repair of MMC is not a complete cure and not free of risk for both mother and fetus, current data clearly demonstrate that open fetal-maternal surgery is to be recommended as novel standard of care when pregnancy is to be continued and when respective criteria for the intervention before birth are met. Undoubtedly, it is imperative to inform expecting mothers about the option of prenatal surgery once their fetus is diagnosed with open spina bifida.
引用
收藏
页码:689 / 697
页数:9
相关论文
共 70 条
[1]   A Randomized Trial of Prenatal versus Postnatal Repair of Myelomeningocele [J].
Adzick, N. Scott ;
Thom, Elizabeth A. ;
Spong, Catherine Y. ;
Brock, John W., III ;
Burrows, Pamela K. ;
Johnson, Mark P. ;
Howell, Lori J. ;
Farrell, Jody A. ;
Dabrowiak, Mary E. ;
Sutton, Leslie N. ;
Gupta, Nalin ;
Tulipan, Noel B. ;
D'Alton, Mary E. ;
Farmer, Diana L. .
NEW ENGLAND JOURNAL OF MEDICINE, 2011, 364 (11) :993-1004
[2]   Open fetal surgery for life-threatening fetal anomalies [J].
Adzick, N. Scott .
SEMINARS IN FETAL & NEONATAL MEDICINE, 2010, 15 (01) :1-8
[3]   Successful fetal surgery for spina bifida [J].
Adzick, NS ;
Sutton, LN ;
Crombleholme, TM ;
Flake, AW .
LANCET, 1998, 352 (9141) :1675-1676
[4]   Correction of hindbrain herniation and anatomy of the vermis after in utero repair of myelomeningocele in sheep [J].
Bouchard, S ;
Davey, MG ;
Rintoul, NE ;
Walsh, DS ;
Rorke, LB ;
Adzick, NS .
JOURNAL OF PEDIATRIC SURGERY, 2003, 38 (03) :451-458
[5]   In utero repair of myelomeningocele: A comparison of endoscopy and hysterotomy [J].
Bruner, JP ;
Tulipan, NB ;
Richards, WO ;
Walsh, WF ;
Boehm, FH ;
Vrabcak, EK .
FETAL DIAGNOSIS AND THERAPY, 2000, 15 (02) :83-88
[6]   Endoscopic coverage of fetal myelomeningocele in utero [J].
Bruner, JP ;
Richards, WO ;
Tulipan, NB ;
Arney, TL .
AMERICAN JOURNAL OF OBSTETRICS AND GYNECOLOGY, 1999, 180 (01) :153-158
[7]   Endoscopic coverage of fetal open myelomeningocele in utero [J].
Bruner, JP ;
Tulipan, NE ;
Richards, WO .
AMERICAN JOURNAL OF OBSTETRICS AND GYNECOLOGY, 1997, 176 (01) :256-257
[8]  
CAMERON AH, 1956, LANCET, V271, P171
[9]   Evidence and Patterns in Lung Response after Fetal Tracheal Occlusion: Clinical Controlled Study [J].
Cannie, Mieke M. ;
Jani, Jacques C. ;
De Keyzer, Frederik ;
Allegaert, Karel ;
Dymarkowski, Steven ;
Deprest, Jan .
RADIOLOGY, 2009, 252 (02) :526-533
[10]   Improvement of motor function and decreased need for postnatal shunting in children who had undergone intrauterine myelomeningocele repair [J].
Carbonari de Faria, Tereza Cristina ;
Cavalheiro, Sergio ;
Hisaba, Wagner Jou ;
Fernandes Moron, Antonio ;
Torloni, Maria Regina ;
Batista de Oliveira, Ana Lucia ;
Borges, Carolina Peixoto .
ARQUIVOS DE NEURO-PSIQUIATRIA, 2013, 71 (9A) :604-608