A missense mutation in zbtb17 blocks the earliest steps of T cell differentiation in zebrafish

被引:10
作者
Lawir, Divine-Fondzenyuy [1 ]
Iwanami, Norimasa [1 ]
Schorpp, Michael [1 ]
Boehm, Thomas [1 ]
机构
[1] Max Planck Inst Immunobiol & Epigenet, Dept Dev Immunol, Stuebeweg 51, D-79108 Freiburg, Germany
关键词
TRANSCRIPTION FACTOR MIZ-1; GENETIC-EVIDENCE; IMMUNE-SYSTEM; B-CELLS; EXPRESSION; THYMUS; MYELOPOIESIS; SUPPRESSOR; FINGERS; IKAROS;
D O I
10.1038/srep44145
中图分类号
O [数理科学和化学]; P [天文学、地球科学]; Q [生物科学]; N [自然科学总论];
学科分类号
07 ; 0710 ; 09 ;
摘要
T cells are an evolutionarily conserved feature of the adaptive immune systems of vertebrates. Comparative studies using evolutionarily distant species hold great promise for unraveling the genetic landscape underlying this process. To this end, we used ENU mutagenesis to generate mutant zebrafish with specific aberrations in early T cell development. Here, we describe the identification of a recessive missense mutation in the transcriptional regulator zbtb17 (Q562K), which affects the ninth zinc finger module of the protein. Homozygous mutant fish exhibit an early block of intrathymic T cell development, as a result of impaired thymus colonization owing to reduced expression of the gene encoding the homing receptor ccr9a, and inefficient T cell differentiation owing to reduced expression of socs1a. Our results reveal the zbtb17-socs1 axis as an evolutionarily conserved central regulatory module of early T cell development of vertebrates.
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页数:11
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