At the X-Roads of Sex and Genetics in Pulmonary Arterial Hypertension

被引:7
作者
Cirulis, Meghan M. [1 ,2 ]
Dodson, Mark W. [1 ,2 ]
Brown, Lynn M. [1 ,2 ]
Brown, Samuel M. [1 ,2 ]
Lahm, Tim [3 ,4 ,5 ]
Elliott, Greg [1 ,2 ]
机构
[1] Univ Utah, Div Pulm Crit Care & Occupat Med, Salt Lake City, UT 84132 USA
[2] Intermt Med Ctr, Div Pulm & Crit Care Med, Salt Lake City, UT 84107 USA
[3] Indiana Univ Sch Med, Dept Med, Div Pulm Crit Care Sleep & Occupat Med, Indianapolis, IN 46202 USA
[4] Richard L Roudebush Vet Affairs Med Ctr, Indianapolis, IN 46202 USA
[5] Indiana Univ Sch Med, Dept Anat Cell Biol & Physiol, Indianapolis, IN 46202 USA
关键词
bone morphogenetic protein receptor type 2; heritable; familial; estrogen; estradiol; penetrance; gender; PAH; RIGHT-VENTRICULAR FUNCTION; SMOOTH-MUSCLE-CELLS; ESTROGEN-RECEPTOR; GERMLINE MUTATIONS; CLINICAL-OUTCOMES; BMPR2; METABOLISM; EXPRESSION; ESTRADIOL; RATS;
D O I
10.3390/genes11111371
中图分类号
Q3 [遗传学];
学科分类号
071007 ; 090102 ;
摘要
Group 1 pulmonary hypertension (pulmonary arterial hypertension; PAH) is a rare disease characterized by remodeling of the small pulmonary arteries leading to progressive elevation of pulmonary vascular resistance, ultimately leading to right ventricular failure and death. Deleterious mutations in the serine-threonine receptor bone morphogenetic protein receptor 2 (BMPR2; a central mediator of bone morphogenetic protein (BMP) signaling) and female sex are known risk factors for the development of PAH in humans. In this narrative review, we explore the complex interplay between the BMP and estrogen signaling pathways, and the potentially synergistic mechanisms by which these signaling cascades increase the risk of developing PAH. A comprehensive understanding of these tangled pathways may reveal therapeutic targets to prevent or slow the progression of PAH.
引用
收藏
页码:1 / 10
页数:10
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