Recombinant adeno-associated virus-mediated alpha-1 antitrypsin gene therapy prevents type I diabetes in NOD mice

被引:87
作者
Song, S
Goudy, K
Campbell-Thompson, M
Wasserfall, C
Scott-Jorgensen, M
Wang, J
Tang, Q
Crawford, JM
Ellis, TM
Atkinson, MA
Flotte, TR
机构
[1] Univ Florida, J Hillis Miller Hlth Ctr, Dept Pharmaceut, Gainesville, FL 32610 USA
[2] Univ Florida, Dept Pathol, Gainesville, FL 32611 USA
[3] Univ Florida, Dept Pediat, Gainesville, FL 32611 USA
[4] Univ Florida, Powell Gene Therapy Ctr, Gainesville, FL 32611 USA
关键词
serpin; alpha; 1; antitrypsin; diabetes; autoimmunity; inflammation;
D O I
10.1038/sj.gt.3302156
中图分类号
Q5 [生物化学]; Q7 [分子生物学];
学科分类号
071010 ; 081704 ;
摘要
Type I diabetes results from an autoimmune destruction of the insulin-producing pancreatic beta cells. Although the exact immunologic processes underlying this disease are unclear, increasing evidence suggests that immunosuppressive, immunoregulatory and anti-inflammatory agents can interrupt the progression of the disease. Alpha 1 antitrypsin (AAT) is a multifunctional serine proteinase inhibitor (serpin) that also displays a wide range of anti-inflammatory properties. To test the ability of AAT to modulate the development of type I diabetes, we performed a series of investigations involving recombinant adeno-associated virus vector (rAAV)-mediated gene delivery of human alpha-1 antitrypsin (hAAT) to nonobese diabetic (NOD) mice. Recombinant AAV-expressing hAAT (rAAV2-CB-AT) was administered intramuscularly to 4-week-old female NOD mice (1 x 10(10) i.u./mouse). A single injection of this vector reduced the intensity of insulitis, the levels of insulin autoantibodies, and the frequency of overt type I diabetes (30% (3/10) at 32 weeks of age versus 70% (7/10) in controls). Transgene expression at the injection sites was confirmed by immunostaining. Interestingly, antibodies against hAAT were present in a majority of the vector-injected mice and circulating hAAT was undetectable when assessed 10 weeks postinjection. This study suggests a potential therapeutic role for AAT in preventing type I diabetes as well as the ability of AAV gene therapy-based approaches to ameliorate disease effectively.
引用
收藏
页码:181 / 186
页数:6
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