Epidemiological studies of spectrin mutations related to hereditary elliptocytosis and spectrin polymorphisms in Benin

被引:38
|
作者
GleleKakai, C
Garbarz, M
Lecomte, MC
Leborgne, S
Galand, C
Bournier, O
Devaux, I
Gautero, H
Zohoun, I
Gallagher, PG
Forget, BG
Dhermy, D
机构
[1] FAC XAVIER BICHAT, INSERM, U409, F-75870 PARIS 18, FRANCE
[2] CTR NATL HOSP & UNIV, COTONOU, BENIN
[3] YALE UNIV, SCH MED, DEPT PEDIAT, NEW HAVEN, CT 06510 USA
[4] YALE UNIV, SCH MED, DEPT INTERNAL MED, NEW HAVEN, CT 06510 USA
[5] YALE UNIV, SCH MED, DEPT GENET, NEW HAVEN, CT 06510 USA
关键词
spectrin; mutation; elliptocytosis; polymorphism;
D O I
10.1046/j.1365-2141.1996.d01-1869.x
中图分类号
R5 [内科学];
学科分类号
1002 ; 100201 ;
摘要
We studied an African population in Benin and discovered an unexpectedly high frequency (1.6%) of hereditary elliptocytosis (HE) among the 1447 subjects studied. In approximately two-thirds of HE individuals we identified molecular defects, primarily those in erythrocyte alpha-spectrin (dupL154, L260P and L207P mutations), as well as a novel mutation of erythrocyte beta-spectrin (beta-W2061R mutation). We also identified the genetic basis of a previously identified protein polymorphism of the alpha III domain of spectrin (R1331I mutation). The genetic background of HE in the African population was studied using a number of polymorphisms of the alpha-spectrin gene, including the alpha III domain polymorphism. These studies suggest that the HE mutations appear to have originated from separate genetic backgrounds in this population.
引用
收藏
页码:57 / 66
页数:10
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