Difficult Therapeutic Decisions in Gorham-Stout Disease-Case Report and Review of the Literature

被引：4
|
作者：
Wojciechowska-Durczynska, Katarzyna [1 ,2 ]
Zygmunt, Arkadiusz [1 ,2 ]
Mikulak, Marta [2 ]
Ludwisiak, Marta [2 ]
Lewinski, Andrzej [1 ,2 ]
机构：
[1] Med Univ Lodz, Dept Endocrinol & Metab Dis, PL-93338 Lodz, Poland
[2] Polish Mothers Mem Hosp, Res Inst, Dept Endocrinol & Metab Dis, PL-93338 Lodz, Poland
来源：
INTERNATIONAL JOURNAL OF ENVIRONMENTAL RESEARCH AND PUBLIC HEALTH | 2022年 / 19卷 / 18期
关键词：
osteolysis; lymphogenesis; zoledronic acid; sirolimus; therapy; OSTEOCLAST FORMATION; BONE-RESORPTION; MECHANISMS; SIROLIMUS; CELLS;
D O I：
10.3390/ijerph191811692
中图分类号：
X [环境科学、安全科学];
学科分类号：
08 ; 0830 ;
摘要：
Gorham-Stout disease (GSD) is a very rare, life-threatening condition characterized by the proliferation of lymphatic vessels and osteolysis. Unfortunately, no standard treatment has been determined for management of GSD. The available therapies are not equally effective and carry substantial side-effects. We report a 42-year-old female with GSD manifested in multifocal osteolysis and chronic chylothorax and ascites. The combined treatment with sirolimus and zoledronic acid due to its synergism of action was introduced. To our knowledge, this is the first Polish case report of adult patients with Gorham-Stout disease.
引用
收藏
页数：8
相关论文
共 50 条
  • [1] Sirolimus on Gorham-Stout disease. Case report
    Garcia, Vanessa
    Alonso-Claudio, Gloria
    Gomez-Hernandez, M-Teresa
    Chamorro, Antonio-J
    Colombia Medica, 2016, 47 (04): : 213 - 216
  • [2] Novel approach of treating Gorham-Stout disease in the humerus - Case report and review of literature
    Ellati, R.
    Attili, A.
    Haddad, H.
    Al-Hussaini, M.
    Shehadeh, A.
    EUROPEAN REVIEW FOR MEDICAL AND PHARMACOLOGICAL SCIENCES, 2016, 20 (03) : 426 - 432
  • [3] Surgical treatment of Gorham-Stout disease combined with scoliosis: a case report and literature review
    Jiao, Yang
    Sun, Heng
    Huang, Yizhen
    Zhao, Junduo
    Huang, Xu'an
    Cai, Haoyu
    Shen, Jianxiong
    BMC MUSCULOSKELETAL DISORDERS, 2024, 25 (01)
  • [4] Gorham-Stout disease of the malleolus: a rare case report
    Zheng, Chuanxi
    Tang, Fan
    Min, Li
    Zhou, Yong
    Luo, Yi
    Tu, Chongqi
    Zhang, Shiquan
    BMC MUSCULOSKELETAL DISORDERS, 2019, 21 (01)
  • [5] Treatment of Gorham-Stout Disease With Zoledronic Acid and Interferon-α: A Case Report and Literature Review
    Kuriyama, Dawn K.
    McElligott, Sean C.
    Glaser, Darryl W.
    Thompson, Karen S.
    JOURNAL OF PEDIATRIC HEMATOLOGY ONCOLOGY, 2010, 32 (08) : 579 - 584
  • [6] Gorham-Stout disease of the mandible: case report and review of literature of a rare type of osteolysis
    Jagtap, Rohan
    Gupta, Swati
    Lamfon, Abdullah
    Ruprecht, Axel
    Schlott, Benjamin
    Hardeman, John
    Kashtwari, Deeba
    ORAL RADIOLOGY, 2020, 36 (04) : 389 - 394
  • [7] Gorham-Stout disease of the malleolus: a rare case report
    Chuanxi Zheng
    Fan Tang
    Li Min
    Yong Zhou
    Yi Luo
    Chongqi Tu
    Shiquan Zhang
    BMC Musculoskeletal Disorders, 21
  • [8] Case Report and Literature Review: Bisphosphonate, Sirolimus, and Atenolol Treatment in a 4-Year-Old Child Diagnosed with Gorham-Stout Disease
    Park, Su Jin
    Yoo, Jae Won
    Ahn, Moon Bae
    PHARMACEUTICALS, 2023, 16 (10)
  • [9] Gorham-Stout disease and multiple cervical lymphangiomas: case report
    Amezquita, Maria Alejandra
    Sua, Luz Fernanda
    Garcia, Carlos Alejandro
    Fernandez-Trujillo, Liliana
    MULTIDISCIPLINARY RESPIRATORY MEDICINE, 2024, 19
  • [10] Surgical treatment of a patient with Gorham-Stout disease of craniovertebral junction: case report and literature review
    Evsyukov, Aleksey
    Kosimshoev, Murodzhon
    Kubetskyi, Yuliy
    Nikitenko, Evgeniy
    Rzaev, Jamil
    BRITISH JOURNAL OF NEUROSURGERY, 2024, 38 (04) : 972 - 977
12345