Critical stenosis of a right ventricle to coronary artery fistula seen at dual-source CT in a newborn with pulmonary atresia and intact ventricular septum

被引:7
作者
Seguela, Pierre-Emmanuel [1 ,2 ]
Houyel, Lucile [2 ]
Loget, Philippe [3 ]
Piot, Jean-Dominique [2 ]
Paul, Jean-Francois [4 ]
机构
[1] Hop Enfants, F-31059 Toulouse 9, France
[2] Ctr Chirurg Marie Lannelongue, Dept Pediat Cardiol, Le Plessis Robinson, France
[3] Ctr Hosp Univ Rennes, Dept Pathol, Rennes, France
[4] Ctr Chirurg Marie Lannelongue, Dept Pediat Radiol, Le Plessis Robinson, France
关键词
Pulmonary atresia with intact ventricular septum; Coronary fistula; Congenital heart disease; Computed tomography;
D O I
10.1007/s00247-011-2068-5
中图分类号
R72 [儿科学];
学科分类号
100202 ;
摘要
We report the case of a newborn with pulmonary atresia with intact ventricular septum and right ventricle-dependent coronary circulation. He died several weeks after a Blalock-Taussig procedure because of a progressive stenosis of the main coronary artery. We present echocardiographic and dual-source CT images of the stenosis, with autopsy correlation. To our knowledge, CT images of this quality have never been reported in a newborn. This case illustrates the extreme difficulty in prognosticating the outcome for these patients and underlines the need for a detailed neonatal coronary mapping to assess right ventricle-dependent coronary circulation.
引用
收藏
页码:1069 / 1072
页数:4
相关论文
共 7 条
[1]   Evaluation of image quality and radiation dose of thoracic and coronary dual-source CT in 110 infants with congenital heart disease [J].
Ben Saad, Moez ;
Rohnean, Adela ;
Sigal-Cinqualbre, Anne ;
Adler, Ghazal ;
Paul, Jean-Francois .
PEDIATRIC RADIOLOGY, 2009, 39 (07) :668-676
[2]   The prevalence of coronary arterial abnormalities in pulmonary atresia with intact ventricular septum and their influence on surgical results [J].
Calder, A. Louise ;
Peebles, Charles R. ;
Occleshaw, Christopher J. .
CARDIOLOGY IN THE YOUNG, 2007, 17 (04) :387-396
[3]   DIAGNOSIS AND MANAGEMENT OF RIGHT VENTRICLE-DEPENDENT CORONARY CIRCULATION IN PULMONARY ATRESIA WITH INTACT VENTRICULAR SEPTUM [J].
GIGLIA, TM ;
MANDELL, VS ;
CONNOR, AR ;
MAYER, JE ;
LOCK, JE .
CIRCULATION, 1992, 86 (05) :1516-1528
[4]   Coronary artery visibility in free-breathing young children with congenital heart disease on cardiac 64-slice CT: dual-source ECG-triggered sequential scan vs. single-source non-ECG-synchronized spiral scan [J].
Goo, Hyun Woo ;
Yang, Dong Hyun .
PEDIATRIC RADIOLOGY, 2010, 40 (10) :1670-1680
[5]   Radiation dose for thoracic and coronary step-and-shoot CT using a 128-slice dual-source machine in infants and small children with congenital heart disease [J].
Paul, Jean-Francois ;
Rohnean, Adela ;
Elfassy, Eric ;
Sigal-Cinqualbre, Anne .
PEDIATRIC RADIOLOGY, 2011, 41 (02) :244-249
[6]   Outcome in infant with pulmonary atresia, intact ventricular septum, and right ventricle-dependent coronary circulation [J].
Powell, AJ ;
Mayer, JE ;
Lang, P ;
Lock, JE .
AMERICAN JOURNAL OF CARDIOLOGY, 2000, 86 (11) :1272-+
[7]   Echocardiographic predictors of coronary artery pathology in pulmonary atresia with intact ventricular septum [J].
Satou, GM ;
Perry, SB ;
Gauvreau, K ;
Geva, T .
AMERICAN JOURNAL OF CARDIOLOGY, 2000, 85 (11) :1319-1324