Pathogenic PSEN1 Thr119Ile Mutation in Two Korean Patients with Early-Onset Alzheimer's Disease

被引:2
作者
Bagyinszky, Eva [1 ]
Lee, Hyon [2 ]
Pyun, Jung Min [3 ,4 ]
Suh, Jeewon [3 ,4 ]
Kang, Min Ju [5 ]
Van Giau Vo [6 ,7 ]
An, Seong Soo A. [7 ]
Park, Kee Hyung [2 ]
Kim, SangYun [3 ,4 ]
机构
[1] Gachon Univ, Dept Ind & Environm Engn, Grad Sch Environm, Seongnam 13120, South Korea
[2] Gachon Univ, Dept Neurol, Gil Med Ctr, Incheon 21565, South Korea
[3] Seoul Natl Univ, Coll Med, Dept Neurol, Seongnam 13620, South Korea
[4] Seoul Natl Univ, Bundang Hosp, Neurocognit Behav Ctr, Seongnam 13620, South Korea
[5] Vet Hlth Serv Med Ctr, Vet Med Res Inst, Dept Neurol, Seoul 05368, South Korea
[6] Duy Tan Univ, Inst Res & Dev, Danang 550000, Vietnam
[7] Gachon Univ, Dept Bionano Technol, Seongnam 13120, South Korea
基金
新加坡国家研究基金会;
关键词
Alzheimer's disease; Thr119Ile mutation; presenilin-1; next generation sequencing; PRESENILIN-1; GENE; PROTEIN; OLIGOMERS; MECHANISM; FAMILY; ROLES; AGE;
D O I
10.3390/diagnostics10060405
中图分类号
R5 [内科学];
学科分类号
1002 ; 100201 ;
摘要
We report a probable pathogenic Thr119Ile mutation in presenilin-1 (PSEN1) in two unrelated Korean patients, diagnosed with early onset Alzheimer's disease (EOAD). The first patient presented with memory decline when she was 64 years old. Magnetic resonance imaging (MRI) scans showed diffuse atrophy in the fronto-parietal regions. In addition, 18F-fludeoxyglucose positron emission tomography (FDG-PET) showed reduced tracer uptake in the parietal and temporal cortices, bilaterally. The second patient developed memory dysfunction at the age of 49, and his mother was also affected. Amyloid positron emission tomography (PET) was positive, but MRI scans did not reveal any atrophy. Targeted NGS and Sanger sequencing identified a heterozygous C to T exchange in PSEN1 exon 5 (c.356C>T), resulting in a p.Thr119Ile mutation. The mutation is located in the conserved HL-I loop, where several Alzheimer's disease (AD) related mutations have been described. Structure analyses suggested that Thr119Ile mutation may result in a significant change inside conservative loop. Additional in vitro studies are needed to estimate the role of the PSEN1 Thr119Ile in AD disease progression.
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页数:10
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