Neuro-Cells therapy improves motor outcomes and suppresses inflammation during experimental syndrome of amyotrophic lateral sclerosis in mice

被引:23
作者
de Munter, Johannes P. J. M. [1 ]
Shafarevich, Igor [2 ,3 ]
Liundup, Alexei [4 ]
Pavlov, Dmitrii [1 ,2 ,3 ,5 ]
Wolters, Erik Ch [1 ]
Gorlova, Anna [1 ,2 ,3 ]
Veniaminova, Ekaterina [1 ,2 ,3 ]
Umriukhin, Aleksei [2 ,3 ]
Kalueff, Allan [6 ,7 ]
Svistunov, Andrei [2 ,3 ,4 ]
Kramer, Boris W. [8 ]
Lesch, Klaus-Peter [1 ,2 ,3 ,9 ]
Strekalova, Tatyana [1 ,2 ,3 ,5 ,9 ]
机构
[1] Maastricht Univ, Sch Mental Hlth & Neurosci, Dept Psychiat & Neuropsychol, Maastricht, Netherlands
[2] Sechenov First Moscow State Med Univ, Lab Psychiat Neurobiol, Inst Mol Med, Moscow, Russia
[3] Sechenov First Moscow State Med Univ, Dept Normal Physiol, Moscow, Russia
[4] Sechenov First Moscow State Med Univ, Inst Regenerat Med, Moscow, Russia
[5] Inst Gen Pathol & Pathophysiol, Lab Cognit Dysfunct, Moscow, Russia
[6] Ural Fed Univ, Fac Biol, Ekaterinburg, Russia
[7] Southwest Univ, Sch Pharm, Chongqing, Peoples R China
[8] Univ Med Ctr MUCM, Dept Pediat, P Debyelaan 25, NL-229 HX Maastricht, Netherlands
[9] Univ Wurzburg, Div Mol Psychiat, Ctr Mental Hlth, Wurzburg, Germany
关键词
amyotrophic lateral sclerosis (ALS); fused in sarcoma (FUS) protein; glycogen-synthase kinase-3 ss (GSK-3 ss); microglia activation; mouse; stem cell therapy; superoxide dismutase-1 (SOD-1) G93A mice; MESENCHYMAL STEM-CELLS; MARROW STROMAL CELLS; INJURED SPINAL-CORD; MOUSE MODEL; TRANSPLANTATION; MUTATIONS; PHENOTYPE; STRESS; TRIAL;
D O I
10.1111/cns.13280
中图分类号
Q189 [神经科学];
学科分类号
071006 ;
摘要
Aims Mutations in DNA/RNA-binding factor (fused-in-sarcoma) FUS and superoxide dismutase-1 (SOD-1) cause amyotrophic lateral sclerosis (ALS). They were reproduced in SOD-1-G93A (SOD-1) and new FUS[1-359]-transgenic (FUS-tg) mice, where inflammation contributes to disease progression. The effects of standard disease therapy and anti-inflammatory treatments were investigated using these mutants. Methods FUS-tg mice or controls received either vehicle, or standard ALS treatment riluzole (8 mg/kg/day), or anti-inflammatory drug a selective blocker of cyclooxygenase-2 celecoxib (30 mg/kg/day) for six weeks, or a single intracerebroventricular (i.c.v.) infusion of Neuro-Cells (a preparation of 1.39 x 10(6) mesenchymal and hemopoietic human stem cells, containing 5 x 10(5) of CD34(+) cells), which showed anti-inflammatory properties. SOD-1 mice received i.c.v.-administration of Neuro-Cells or vehicle. Results All FUS-tg-treated animals displayed less marked reductions in weight gain, food/water intake, and motor deficits than FUS-tg-vehicle-treated mice. Neuro-Cell-treated mutants had reduced muscle atrophy and lumbar motor neuron degeneration. This group but not celecoxib-FUS-tg-treated mice had ameliorated motor performance and lumbar expression of microglial activation marker, ionized calcium-binding adapter molecule-1 (Iba-1), and glycogen-synthase-kinase-3 ss (GSK-3 ss). The Neuro-Cells-treated-SOD-1 mice showed better motor functions than vehicle-treated-SOD-1 group. Conclusion The neuropathology in FUS-tg mice is sensitive to standard ALS treatments and Neuro-Cells infusion. The latter improves motor outcomes in two ALS models possibly by suppressing microglial activation.
引用
收藏
页码:504 / 517
页数:14
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