Responsiveness of Daytime Sleepiness and Fatigue Scales in Myotonic Dystrophy Type 1

被引：1

作者：

Laberge, Luc ^{[1
,2
,3
,4
,5
]}

Gallais, Benjamin ^{[1
,2
,3
,4
,5
]}

Auclair, Julie ^{[1
]}

Dauvilliers, Yves ^{[6
]}

Cote, Isabelle ^{[4
]}

Mathieu, Jean ^{[3
,4
,5
]}

Gagnon, Cynthia ^{[3
,4
,5
]}

机构：

[1] Cegep Jonquiere, ECOBES Rech & Transfert, 2505 Rue St Hubert, Jonquiere, PQ G7X 7W2, Canada

[2] Univ Quebec Chicoutimi, Dept Sci Sante, Chicoutimi, PQ, Canada

[3] Univ Sherbrooke, Fac Med & Sci Sante, Sherbrooke, PQ, Canada

[4] Ctr Integre Univ Sante & Serv Sociaux Saguenay La, Grp Rech Interdisciplinaire Sur Malad Neuromuscul, Chicoutimi, PQ, Canada

[5] Univ Sherbrooke, Ctr Rech Charles Le Moyne, Ctr Integre Univ Saguenay Lac St Jean Sur Innovat, Sherbrooke, PQ, Canada

[6] Hop Gui de Chauliac, Dept Neurol, Montpellier, France

来源：

CANADIAN JOURNAL OF NEUROLOGICAL SCIENCES | 2022年 / 49卷 / 02期

基金：

加拿大健康研究院;

关键词：

Myotonic dystrophy; Sleep; Fatigue; Responsiveness to change;

D O I：

10.1017/cjn.2021.77

中图分类号：

R74 [神经病学与精神病学];

学科分类号：

摘要：

Daytime sleepiness and fatigue are prominent symptoms of myotonic dystrophy type 1 (DM1) that can be amenable to treatment in the context of randomized controlled trials. No study has yet documented whether self-reported measures of daytime sleepiness and fatigue can detect change over time and the meaning of this change. The aim was to explore indicators of responsiveness to change and interpretability for the Daytime Sleepiness Scale and the Fatigue Severity Scale in 115 DM1 prospectively followed patients. Results suggest that these two self-reported questionnaires are sufficiently sensitive to detect changes beyond expected measurement error over time in this population.

引用

页码：287 / 290

页数：4

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