A De Novo Mutation in DYRK1A Causes Syndromic Intellectual Disability: A Chinese Case Report

被引:10
作者
Qiao, Fengchang [1 ]
Shao, Binbin [1 ]
Wang, Chen [1 ]
Wang, Yan [1 ]
Zhou, Ran [1 ]
Liu, Gang [1 ]
Meng, Lulu [1 ]
Hu, Ping [1 ]
Xu, Zhengfeng [1 ]
机构
[1] Nanjing Med Univ, Nanjing Matern & Child Hlth Care Hosp, Womens Hosp, Dept Prenatal Diag, Nanjing, Jiangsu, Peoples R China
基金
中国国家自然科学基金; 国家重点研发计划;
关键词
DYRK1A; intellectual disability; microcephaly; nonsense mutation; whole-exome sequencing; DOWN-SYNDROME; HUMAN HOMOLOG; HAPLOINSUFFICIENCY; MNB/DYRK1A; GENE; DIAGNOSIS; DELETION; KINASE; AUTISM; MAPS;
D O I
10.3389/fgene.2019.01194
中图分类号
Q3 [遗传学];
学科分类号
071007 ; 090102 ;
摘要
Autosomal dominant mental retardation-7 (MRD7) is a rare anomaly, characterized by severe intellectual disability, feeding difficulties, behavior abnormalities, and distinctive facial features, including microcephaly, deep-set eyes, large simple ears, and a pointed or bulbous nasal tip. Some studies show that the disorder has a close correlation with variants in DYRK1A. Herein we described a Chinese girl presenting typical clinical features diagnosed at 4 years old. Whole-exome sequencing of the familial genomic DNA identified a novel mutation c.930C > A (p.Tyr310*) in exon 7 of DYRK1A in the proband. The nonsense mutation was predicted to render the truncation of the protein. Our results suggested that the de novo heterozygous mutation in DYRK1A was responsible for the MRD7 in this Chinese family, which both extended the knowledge of mutation spectrum in MRD7 patients and highlighted the clinical application of exome sequencing.
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