Molecular Basis, Diagnostic Challenges and Therapeutic Approaches of Alport Syndrome: A Primer for Clinicians

被引:10
作者
Martinez-Pulleiro, Raquel [1 ,2 ]
Garcia-Murias, Maria [1 ,2 ]
Fidalgo-Diaz, Manuel [3 ]
Angel Garcia-Gonzalez, Miguel [1 ,2 ,4 ]
机构
[1] Complexo Hosp Santiago de Compostela CHUS, Inst Invest Sanitaria Santiago IDIS, Lab Nefrol 11, Grp Xenet & Biol Desenvolvemento Enfermidades Ren, Santiago De Compostela 15706, Spain
[2] Grp Med Xenom GMX, Santiago De Compostela 15706, Spain
[3] Complexo Hosp Univ Santiago CHUS, Dept Nefrol, Santiago De Compostela 15706, Spain
[4] Complexo Hosp Santiago de Compostela CHUS, Fdn Publ Galega Med Xenom SERGAS, Santiago De Compostela 15706, Spain
关键词
Alport syndrome; hereditary kidney disease; chronic kidney disease; collagen; COL4A; GLOMERULAR-BASEMENT-MEMBRANE; GENOTYPE-PHENOTYPE CORRELATIONS; KIDNEY-DISEASE PROGRESSION; DELAYS RENAL-FAILURE; KNOCKOUT MOUSE MODEL; NATURAL-HISTORY; COL4A3; KNOCKOUT; DIGENIC INHERITANCE; RAAS INHIBITION; MESANGIAL CELLS;
D O I
10.3390/ijms222011063
中图分类号
Q5 [生物化学]; Q7 [分子生物学];
学科分类号
071010 ; 081704 ;
摘要
Alport syndrome is a genetic and hereditary disease, caused by mutations in the type IV collagen genes COL4A3, COL4A4 and COL4A5, that affects the glomerular basement membrane of the kidney. It is a rare disease with an underestimated prevalence. Genetic analysis of population cohorts has revealed that it is the second most common inherited kidney disease after polycystic kidney disease. Renal involvement is the main manifestation, although it may have associated extrarenal manifestations such as hearing loss or ocular problems. The degree of expression of the disease changes according to the gene affected and other factors, known or yet to be known. The pathophysiology is not yet fully understood, although some receptors, pathways or molecules are known to be linked to the disease. There is also no specific treatment for Alport syndrome; the most commonly used are renin-angiotensin-aldosterone system inhibitors. In recent years, diagnosis has come a long way, thanks to advances in DNA sequencing technologies such as next-generation sequencing (NGS). Further research at the genetic and molecular levels in the future will complete the partial vision of the pathophysiological mechanism that we have, and will allow us to better understand what is happening and how to solve it.
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页数:18
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