Huntington's disease: from molecular pathogenesis to clinical treatment

被引:1191
|
作者
Ross, Christopher A. [1 ,2 ,3 ,4 ]
Tabrizi, Sarah J. [5 ]
机构
[1] Johns Hopkins Univ, Sch Med, Div Neurobiol, Dept Psychiat, Baltimore, MD 21287 USA
[2] Johns Hopkins Univ, Sch Med, Dept Neurol, Baltimore, MD 21287 USA
[3] Johns Hopkins Univ, Sch Med, Dept Pharmacol, Baltimore, MD 21287 USA
[4] Johns Hopkins Univ, Sch Med, Program Cellular & Mol Med, Baltimore, MD 21287 USA
[5] UCL Inst Neurol, Dept Neurodegenerat Dis, London, England
来源
LANCET NEUROLOGY | 2011年 / 10卷 / 01期
基金
英国惠康基金; 英国医学研究理事会;
关键词
HISTONE DEACETYLASE INHIBITORS; UBIQUITIN-PROTEASOME SYSTEM; INCLUSION-BODY FORMATION; R6/2 MOUSE MODEL; AGE-OF-ONSET; MUTANT-HUNTINGTIN; NEURODEGENERATIVE DISEASES; IN-VIVO; POLYGLUTAMINE AGGREGATION; MITOCHONDRIAL DYSFUNCTION;
D O I
10.1016/S1474-4422(10)70245-3
中图分类号
R74 [神经病学与精神病学];
学科分类号
摘要
Huntington's disease is a progressive, fatal, neurodegenerative disorder caused by an expanded CAG repeat in the huntingtin gene, which encodes an abnormally long polyglutamine repeat in the huntingtin protein. Huntington's disease has served as a model for the study of other more common neurodegenerative disorders, such as Alzheimer's disease and Parkinson's disease. These disorders all share features including: delayed onset; selective neuronal vulnerability, despite widespread expression of disease-related proteins during the whole lifetime; abnormal protein processing and aggregation; and cellular toxic effects involving both cell autonomous and cell-cell interaction mechanisms. Pathogenic pathways of Huntington's disease are beginning to be unravelled, offering targets for treatments. Additionally, predictive genetic testing and findings of neuroimaging studies show that, as in some other neurodegenerative disorders, neurodegeneration in affected individuals begins many years before onset of diagnosable signs and symptoms of Huntington's disease, and it is accompanied by subtle cognitive, motor, and psychiatric changes (so-called prodromal disease). Thus, Huntington's disease is also emerging as a model for strategies to develop therapeutic interventions, not only to slow progression of manifest disease but also to delay, or ideally prevent, its onset.
引用
收藏
页码:83 / 98
页数:16
相关论文
共 50 条
  • [31] Myelin breakdown and iron changes in Huntington's disease: Pathogenesis and treatment implications
    Bartzokis, George
    Lu, Po H.
    Tishler, Todd A.
    Fong, Sophia M.
    Oluwadara, Bolanle
    Finn, J. Paul
    Huang, Danny
    Bordelon, Yvette
    Mintz, Jim
    Perlman, Susan
    NEUROCHEMICAL RESEARCH, 2007, 32 (10) : 1655 - 1664
  • [32] Myelin Breakdown and Iron Changes in Huntington’s Disease: Pathogenesis and Treatment Implications
    George Bartzokis
    Po H. Lu
    Todd A. Tishler
    Sophia M. Fong
    Bolanle Oluwadara
    J. Paul Finn
    Danny Huang
    Yvette Bordelon
    Jim Mintz
    Susan Perlman
    Neurochemical Research, 2007, 32 : 1655 - 1664
  • [33] Clinical experience with risperidone and memantine in the treatment of Huntington's disease
    Cankurtaran, Eylem Sahin
    Ozalp, Elvan
    Soygur, Haldun
    Cakir, Aysegul
    JOURNAL OF THE NATIONAL MEDICAL ASSOCIATION, 2006, 98 (08) : 1353 - 1355
  • [34] Treatment of Huntington’s Disease
    Samuel Frank
    Neurotherapeutics, 2014, 11 : 153 - 160
  • [35] Treatment of Huntington's Disease
    Frank, Samuel
    NEUROTHERAPEUTICS, 2014, 11 (01) : 153 - 160
  • [36] Clinical determinants that influence a later molecular diagnosis of Huntington's Disease
    Munuzuri-Camacho, M.
    Garcia-Romero, D.
    Esquivel-Zapata, O.
    Cervantes-Arriaga, A.
    Davila, D.
    Martinez-Ruano, L.
    Medrano, A. Hernandez
    Tellez, H.
    Abundes, A.
    Martinez, C.
    Castro, F.
    Ortega-Bolanos, L.
    Matuk, Y.
    Rodriguez Violante, M.
    EUROPEAN JOURNAL OF NEUROLOGY, 2021, 28 : 787 - 787
  • [37] Pathogenesis of leukodystrophy for Krabbe disease: Molecular mechanism and clinical treatment
    Sakai, Norio
    BRAIN & DEVELOPMENT, 2009, 31 (07): : 485 - 487
  • [38] Alzheimer's Disease: Clinical features, pathogenesis, and treatment
    Rathmann, Kaye L.
    Conner, Christopher S.
    ANNALS OF PHARMACOTHERAPY, 2007, 41 (09) : 1499 - 1504
  • [39] Marfan syndrome: from molecular pathogenesis to clinical treatment
    Ramirez, Francesco
    Dietz, Harry C.
    CURRENT OPINION IN GENETICS & DEVELOPMENT, 2007, 17 (03) : 252 - 258
  • [40] Mitochondria and Huntington's Disease Pathogenesis Insight from Genetic and Chemical Models
    Browne, Susan E.
    MITOCHONDRIA AND OXIDATIVE STRESS IN NEURODEGENERATIVE DISORDERS, 2008, 1147 : 358 - 382