Small Molecule Anion Carriers Correct Abnormal Airway Surface Liquid Properties in Cystic Fibrosis Airway Epithelia

被引:25
作者
Gianotti, Ambra [1 ]
Capurro, Valeria [1 ,4 ]
Delpiano, Livia [1 ]
Mielczarek, Marcin [2 ]
Garcia-Valverde, Maria [2 ]
Carreira-Barral, Israel [2 ]
Ludovico, Alessandra [3 ]
Fiore, Michele [3 ]
Baroni, Debora [3 ]
Moran, Oscar [3 ]
Quesada, Roberto [2 ]
Caci, Emanuela [1 ]
机构
[1] IRCSS Ist Giannina Gaslini, UOC Genet Med, I-16145 Genoa, Italy
[2] Univ Burgos, Fac Ciencias, Dept Quim, Burgos 09001, Spain
[3] CNR, Ist Biofis, I-16149 Genoa, Italy
[4] Newcastle Univ, Biosci Inst, Newcastle Upon Tyne NE1 7RU, Tyne & Wear, England
基金
欧盟地平线“2020”;
关键词
cystic fibrosis; anionophore; bronchial epithelial cells culture; ion transport; periciliar mucus properties; CHLORIDE TRANSPORT; PARTICLE-TRACKING; CFTR; PATHOGENESIS; CHANNEL; CELLS;
D O I
10.3390/ijms21041488
中图分类号
Q5 [生物化学]; Q7 [分子生物学];
学科分类号
071010 ; 081704 ;
摘要
Cystic fibrosis (CF) is a genetic disease characterized by the lack of cystic fibrosis transmembrane conductance regulator (CFTR) protein expressed in epithelial cells. The resulting defective chloride and bicarbonate secretion and imbalance of the transepithelial homeostasis lead to abnormal airway surface liquid (ASL) composition and properties. The reduced ASL volume impairs ciliary beating with the consequent accumulation of sticky mucus. This situation prevents the normal mucociliary clearance, favouring the survival and proliferation of bacteria and contributing to the genesis of CF lung disease. Here, we have explored the potential of small molecules capable of facilitating the transmembrane transport of chloride and bicarbonate in order to replace the defective transport activity elicited by CFTR in CF airway epithelia. Primary human bronchial epithelial cells obtained from CF and non-CF patients were differentiated into a mucociliated epithelia in order to assess the effects of our compounds on some key properties of ASL. The treatment of these functional models with non-toxic doses of the synthetic anionophores improved the periciliary fluid composition, reducing the fluid re-absorption, correcting the ASL pH and reducing the viscosity of the mucus, thus representing promising drug candidates for CF therapy.
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页数:14
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