Molecular Pathophysiological Mechanisms in Huntington's Disease

被引:65
作者
Jurcau, Anamaria [1 ,2 ]
机构
[1] Univ Oradea, Fac Med & Pharm, Dept Psychoneurosci & Rehabil, Oradea 410073, Romania
[2] Clin Emergency Cty Hosp Oradea, Neurol Ward 3, Oradea 410169, Romania
关键词
Huntington's disease; mutant huntingtin; animal models; excitotoxicity; transcriptional dysregulation; proteostasis; mitochondrial dysfunction; oxidative stress; brain-derived neurotrophic factor; NMDA RECEPTOR FUNCTION; AGE-OF-ONSET; MUTANT HUNTINGTIN; MOUSE MODEL; AXONAL-TRANSPORT; CAG REPEAT; WILD-TYPE; INTRANUCLEAR INCLUSIONS; NEURONAL VULNERABILITY; CAENORHABDITIS-ELEGANS;
D O I
10.3390/biomedicines10061432
中图分类号
Q5 [生物化学]; Q7 [分子生物学];
学科分类号
071010 ; 081704 ;
摘要
Huntington's disease is an inherited neurodegenerative disease described 150 years ago by George Huntington. The genetic defect was identified in 1993 to be an expanded CAG repeat on exon 1 of the huntingtin gene located on chromosome 4. In the following almost 30 years, a considerable amount of research, using mainly animal models or in vitro experiments, has tried to unravel the complex molecular cascades through which the transcription of the mutant protein leads to neuronal loss, especially in the medium spiny neurons of the striatum, and identified excitotoxicity, transcriptional dysregulation, mitochondrial dysfunction, oxidative stress, impaired proteostasis, altered axonal trafficking and reduced availability of trophic factors to be crucial contributors. This review discusses the pathogenic cascades described in the literature through which mutant huntingtin leads to neuronal demise. However, due to the ubiquitous presence of huntingtin, astrocytes are also dysfunctional, and neuroinflammation may additionally contribute to Huntington's disease pathology. The quest for therapies to delay the onset and reduce the rate of Huntington's disease progression is ongoing, but is based on findings from basic research.
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页数:35
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