Clinical data analysis of genotypes and phenotypes of deafness gene mutations in newborns: A retrospective study

被引:5
作者
Du, Yating [1 ]
Huang, Lihui [1 ]
Wang, Xueyao [1 ]
Cui, Qingjia [1 ,2 ]
Cheng, Xiaohua [1 ]
Zhao, Liping [1 ]
Ni, Tingting [1 ]
机构
[1] Capital Med Univ, Beijing Tongren Hosp, Beijing Inst Otolaryngol, Key Lab Otolaryngol Head & Neck Surg,Minist Educ, 17 Hougou Lane,Chongnei St, Beijing 100005, Peoples R China
[2] Capital Med Univ, Beijing Rehabil Hosp, Rehabil Ctr Otolaryngol Head & Neck Surg, Beijing, Peoples R China
基金
北京市自然科学基金;
关键词
Gene; screening; GJB2; SLC26A4; hearing loss; ENLARGED VESTIBULAR AQUEDUCT; NONSYNDROMIC HEARING-LOSS; PENDRED-SYNDROME; SLC26A4; MUTATIONS; GJB2; SPECTRUM; FREQUENCIES;
D O I
10.5582/bst.2017.01070
中图分类号
Q [生物科学];
学科分类号
07 ; 0710 ; 09 ;
摘要
We retrospectively analyzed newborns with deafness gene mutations and summarized the relationship between genotype and phenotype to provide a basis for genetic counseling. We studied 582 subjects positive for deafness gene mutations that were treated in the otology outpatient department of Beijing Tongren Hospital, Capital Medical University, between April 2012 and April 2016. The subjects were divided into 3 categories: a diagnosed group (group A), which was further subdivided into subgroups A1 (homozygous and compound heterozygous GJB2 mutations) and A2 (homozygous and compound heterozygous SLC26A4 mutations); a drug-induced deafness group (group B, mitochondrial (Mt) gene mutations); and a mutation carrier group (group C), which was further subdivided into the subgroups C1 (GJB2 heterozygous mutations), C2 (SLC26A4 heterozygous mutations), C3 (GJB3 heterozygous mutations), and C4 (double gene mutations). Partial sequences positive for GJB2 or SLC26A4 were sequenced and analyzed for mutations. Subjects underwent otoscopic examination and comprehensive audiological evaluation, and temporal bone computerized tomography and/or inner ear magnetic resonance imaging were performed. GJB2 235delC was the most common mutation locus. The highest proportion of deafness detected during universal newborn hearing screening was for drug-induced deafness, whereas the lowest was for the diagnosed group. GJB2 gene mutations mainly resulted in flat-type, profound-to-severe sensorineural hearing loss (SNHL). SLC26A4 gene mutation was mainly associated with high-frequency drop-type and profound-severe SNHL and was closely related to enlargement of the vestibular aqueduct.
引用
收藏
页码:460 / 468
页数:9
相关论文
共 38 条
  • [1] Pendred syndrome, DFNB4, and PDS/SCL26A4 identification of eight novel mutations and possible genotype-phenotype correlations
    Campbell, C
    Cucci, RA
    Prasad, S
    Green, GE
    Edeal, JB
    Galer, CE
    Karniski, LP
    Sheffield, VC
    Smith, RJH
    [J]. HUMAN MUTATION, 2001, 17 (05) : 403 - 411
  • [2] Hypo-Functional SLC26A4 Variants Associated with Nonsyndromic Hearing Loss and Enlargement of the Vestibular Aqueduct: Genotype-Phenotype Correlation or Coincidental Polymorphisms?
    Choi, Byung Yoon
    Stewart, Andrew K.
    Madeo, Anne C.
    Pryor, Shannon P.
    Lenhard, Suzanne
    Kittles, Rick
    Eisenman, David
    Kim, H. Jeffrey
    Niparko, John
    Thomsen, James
    Arnos, Kathleen S.
    Nance, Walter E.
    King, Kelly A.
    Zalewski, Christopher K.
    Brewer, Carmen C.
    Shawker, Thomas
    Reynolds, James C.
    Butman, John A.
    Karniski, Lawrence P.
    Alper, Seth L.
    Griffith, Andrew J.
    [J]. HUMAN MUTATION, 2009, 30 (04) : 599 - 608
  • [3] The prevalence of the 235delC GJB2 mutation in a Chinese deaf population
    Dai, Pu
    Yu, Fei
    Han, Bing
    Yuan, Yongyi
    Li, Qi
    Wang, Guojian
    Liu, Xin
    He, Jia
    Huang, Deliang
    Kang, Dongyang
    Zhang, Xin
    Yuan, Huijun
    Schmitt, Eric
    Han, Dongyi
    Wong, Lee-Jun
    [J]. GENETICS IN MEDICINE, 2007, 9 (05) : 283 - 289
  • [4] Dai Pu, 2007, Zhonghua Er Bi Yan Hou Tou Jing Wai Ke Za Zhi, V42, P804
  • [5] [代志瑶 Dai Zhiyao], 2014, [中华耳科学杂志, Chinese Journal of Otology], V12, P34
  • [6] Analysis of p. V37I compound heterozygous mutations in the GJB2 gene in Chinese infants and young children
    Du, Yating
    Huang, Lihui
    Cheng, Xiaohua
    Zhao, Liping
    Ruan, Yu
    Ni, Tingting
    [J]. BIOSCIENCE TRENDS, 2016, 10 (03) : 220 - 226
  • [7] Pendred syndrome is caused by mutations in a putative sulphate transporter gene (PDS)
    Everett, LA
    Glaser, B
    Beck, JC
    Idol, JR
    Buchs, A
    Heyman, M
    Adawi, F
    Hazani, E
    Nassir, E
    Baxevanis, AD
    Sheffield, VC
    Green, ED
    [J]. NATURE GENETICS, 1997, 17 (04) : 411 - 422
  • [8] Genetic testing to identify deaf newborns
    Green, GE
    Smith, RJH
    Bent, JP
    Cohn, ES
    [J]. JAMA-JOURNAL OF THE AMERICAN MEDICAL ASSOCIATION, 2000, 284 (10): : 1245 - 1245
  • [9] Han Y, 2012, YI XUE ZONG SHU, V18, P2774
  • [10] Huang Li-hui, 2006, Zhonghua Er Bi Yan Hou Tou Jing Wai Ke Za Zhi, V41, P331