Iron Overload in an HFE Heterozygous Carrier: A Case Report and Literature Review

被引:8
作者
Turbiville, Donald [1 ]
Du, Xiaotang [2 ]
Yo, Jacob [2 ]
Jana, Bagi R. [3 ]
Dong, Jianli [2 ]
机构
[1] Univ Texas Med Branch, Sch Med, Galveston, TX 77555 USA
[2] Univ Texas Med Branch, Dept Pathol, Galveston, TX 77555 USA
[3] Univ Texas Med Branch, Dept Internal Med, Galveston, TX 77555 USA
关键词
hereditary hemochromatosis; HFE; heterozygous mutation; autosomal recessive; haploinsufficiency; iron overload; HEREDITARY HEMOCHROMATOSIS; MUTATIONS; DIAGNOSIS; PROBANDS;
D O I
10.1093/labmed/lmy065
中图分类号
R446 [实验室诊断]; R-33 [实验医学、医学实验];
学科分类号
1001 ;
摘要
Hereditary hemochromatosis (HH) is an autosomal recessive disorder of iron metabolism characterized by increased iron absorption and tissue deposition. Three loss-of-function mutations in the hemochromatosis gene (HFE), namely, C282Y (c.845G>A), H63D (c.187C>G), and S65C (c.193A>T), account for the vast majority of HH cases. These mutations cause alterations in HFE membrane expression, structure, and/or activity, leading to dysregulation of iron absorption. It is well established that the phenotypic expression of HFE mutations varies markedly. Herein, we describe a 64-year-old Caucasian woman with a reported history of hemochromatosis. The father of the patient had died of complications due to iron overload. Testing of HFE codon C282Y, H63D, and S65C mutations showed heterozygous C282Y. The patient had significantly elevated transferrin saturation (TS) and serum ferritin (SF) levels. Her liver function test results showed elevated alanine transaminase (ALT) and aspartate aminotransferase (AST) levels. The patient has been treated with regular phlebotomy to prevent the clinical manifestations of hemochromatosis.
引用
收藏
页码:212 / 217
页数:6
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