Human CNS barrier-forming organoids with cerebrospinal fluid production

被引:300
作者
Pellegrini, Laura [1 ]
Bonfio, Claudia [1 ]
Chadwick, Jessica [1 ]
Begum, Farida [1 ]
Skehel, Mark [1 ]
Lancaster, Madeline A. [1 ]
机构
[1] MRC Lab Mol Biol, Francis Crick Ave, Cambridge CB2 0QH, England
基金
欧洲研究理事会; 英国医学研究理事会;
关键词
CENTRAL-NERVOUS-SYSTEM; CHOROID-PLEXUS; ALZHEIMERS-DISEASE; PROTEOMIC ANALYSIS; MATRIX METALLOPROTEINASES; CEREBRAL ORGANOIDS; APOLIPOPROTEIN-E; CSF BIOMARKER; TUMOR-MARKERS; SPINAL-FLUID;
D O I
10.1126/science.aaz5626
中图分类号
O [数理科学和化学]; P [天文学、地球科学]; Q [生物科学]; N [自然科学总论];
学科分类号
07 ; 0710 ; 09 ;
摘要
Cerebrospinal fluid (CSF) is a vital liquid, providing nutrients and signaling molecules and clearing out toxic by-products from the brain. The CSF is produced by the choroid plexus (ChP), a protective epithelial barrier that also prevents free entry of toxic molecules or drugs from the blood. Here, we establish human ChP organoids with a selective barrier and CSF-like fluid secretion in self-contained compartments. We show that this in vitro barrier exhibits the same selectivity to small molecules as the ChP in vivo and that ChP-CSF organoids can predict central nervous system (CNS) permeability of new compounds. The transcriptomic and proteomic signatures of ChP-CSF organoids reveal a high degree of similarity to the ChP in vivo. Finally, the intersection of single-cell transcriptomics and proteomic analysis uncovers key human CSF components produced by previously unidentified specialized epithelial subtypes.
引用
收藏
页码:159 / +
页数:58
相关论文
共 130 条
[1]   Increased Cerebrospinal Fluid Level of Insulin-like Growth Factor-II in Male Patients with Alzheimer's Disease [J].
Aberg, Daniel ;
Johansson, Per ;
Isgaard, Jorgen ;
Wallin, Anders ;
Johansson, Jan-Ove ;
Andreasson, Ulf ;
Blennow, Kaj ;
Zetterberg, Henrik ;
Aberg, N. David ;
Svensson, Johan .
JOURNAL OF ALZHEIMERS DISEASE, 2015, 48 (03) :637-646
[2]   Osteopontin (OPN) as a CSF and blood biomarker for multiple sclerosis: A systematic review and meta-analysis [J].
Agah, Elmira ;
Zardoui, Arshia ;
Saghazadeh, Amene ;
Ahmadi, Mona ;
Tafakhori, Abbas ;
Rezaei, Nima .
PLOS ONE, 2018, 13 (01)
[3]   Biomarkers in Spinal Cord Injury: Prognostic Insights and Future Potentials [J].
Albayar, Ahmed A. ;
Roche, Abigail ;
Swiatkowski, Przemyslaw ;
Antar, Sarah ;
Ouda, Nouran ;
Emara, Eman ;
Smith, Douglas H. ;
Ozturk, Ali K. ;
Awad, Basem I. .
FRONTIERS IN NEUROLOGY, 2019, 10
[4]   Blood-Brain Barrier Disruption and Intra-Arterial Methotrexate-Based Therapy for Newly Diagnosed Primary CNS Lymphoma: A Multi-Institutional Experience [J].
Angelov, Lilyana ;
Doolittle, Nancy D. ;
Kraemer, Dale F. ;
Siegal, Tali ;
Barnett, Gene H. ;
Peereboom, David M. ;
Stevens, Glen ;
McGregor, John ;
Jahnke, Kristoph ;
Lacy, Cynthia A. ;
Hedrick, Nancy A. ;
Shalom, Edna ;
Ference, Sandra ;
Bell, Susan ;
Sorenson, Lisa ;
Tyson, Rose Marie ;
Haluska, Marianne ;
Neuwelt, Edward A. .
JOURNAL OF CLINICAL ONCOLOGY, 2009, 27 (21) :3503-3509
[5]   Role of beta-2-microglobulin as a biomarker in very preterm and extremely preterm infants with CNS inflammation [J].
Batista Munoz, Albert ;
Hadley, Stephanie ;
Iriondo Sanz, Marti ;
Agut Quijano, Thais ;
Camprubi Camprubi, Marta .
PLOS ONE, 2019, 14 (05)
[6]   PLASMA-LEVELS OF LEVODOPA AND ITS MAIN METABOLITES IN PARKINSONIAN-PATIENTS AFTER CONVENTIONAL AND CONTROLLED-RELEASE LEVODOPA-CARBIDOPA ASSOCIATIONS [J].
BENETELLO, P ;
FURLANUT, M ;
ZARA, G ;
BARALDO, M ;
HASSAN, E .
EUROPEAN NEUROLOGY, 1993, 33 (01) :69-73
[7]   Statistical issues in first-in-human studies on BIA 10=2474: Neglected comparison of protocol against practice [J].
Bird, Sheila M. ;
Bailey, Rosemary A. ;
Grieve, Andrew P. ;
Senn, Stephen .
PHARMACEUTICAL STATISTICS, 2017, 16 (02) :100-106
[8]   Cerebrospinal Fluid Matrix Metalloproteinases and Tissue Inhibitor of Metalloproteinases in Combination with Subcortical and Cortical Biomarkers in Vascular Dementia and Alzheimer's Disease [J].
Bjerke, Maria ;
Zetterberg, Henrik ;
Edman, Ake ;
Blennow, Kaj ;
Wallin, Anders ;
Andreasson, Ulf .
JOURNAL OF ALZHEIMERS DISEASE, 2011, 27 (03) :665-676
[9]   Insulin-Like Growth Factor Binding Protein 2 Is Associated With Biomarkers of Alzheimer's Disease Pathology and Shows Differential Expression in Transgenic Mice [J].
Bonham, Luke W. ;
Geier, Ethan G. ;
Steele, Natasha Z. R. ;
Holland, Dominic ;
Miller, Bruce L. ;
Dale, Anders M. ;
Desikan, Rahul S. ;
Yokoyama, Jennifer S. .
FRONTIERS IN NEUROSCIENCE, 2018, 12
[10]   Scientists in the dark after fatal French clinical trial [J].
Butler, Declan ;
Callaway, Ewen .
NATURE, 2016, 529 (7586) :263-264