Novel ACTG1 mutation causing autosomal dominant non-syndromic hearing impairment in a Chinese family

被引:28
作者
Liu, Ping [1 ]
Li, Hu [2 ]
Ren, Xiang [1 ]
Mao, Haiyan [2 ]
Zhu, Qihui [1 ]
Zhu, Zhengfeng [2 ]
Yang, Rong [1 ]
Yuan, Wenlin [2 ]
Liu, Jingyu [1 ]
Wang, Qing [1 ]
Liu, Mugen [1 ]
机构
[1] Huazhong Univ Sci & Technol, Coll Life Sci & Technol, Ctr Human Genome Res, Key Lab Mol Biophys Minist Educ, Wuhan 430074, Peoples R China
[2] Fourth Peoples Hosp Yancheng, Jiangsu 224000, Peoples R China
基金
中国国家自然科学基金;
关键词
non-syndromic hearing impairment (NSHI); ACTG1; linkage; sequence analysis; restriction fragment length polymorphism (RFLP) analysis;
D O I
10.1016/S1673-8527(08)60075-2
中图分类号
Q5 [生物化学]; Q7 [分子生物学];
学科分类号
071010 ; 081704 ;
摘要
The gamma-actin (ACTG1) gene is a cytoplasmic nonmuscle actin gene, which encodes a major cytoskeletal protein in the sensory hair cells of the cochlea. Mutations in ACTG1 were found to cause autosomal dominant, progressive, sensorineural hearing loss linked to the DFNA 20/26 locus on chromosome 17q25.3 in European and American families, respectively. In this study, a novel missense mutation (c.364A>G; p.I122V) co-segregated with the affected individuals in the family and did not exist in the unaffected family members and 150 unrelated normal controls. The alteration of residue Ile122 was predicted to damage its interaction with actin-binding proteins, which may cause disruption of hair cell organization and function. These findings strongly suggested that the I122V mutation in ACTG1 caused autosomal dominant non-syndromic hearing impairment in a Chinese family and expanded the spectrum of ACTG1 mutations causing hearing loss.
引用
收藏
页码:553 / 558
页数:6
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