Unbiased screen for interactors of leucine-rich repeat kinase 2 supports a common pathway for sporadic and familial Parkinson disease

被引:275
作者
Beilina, Alexandria [1 ]
Rudenko, Iakov N. [1 ]
Kaganovich, Alice [1 ]
Civiero, Laura [4 ]
Chau, Hien [5 ]
Kalia, Suneil K. [6 ]
Kalia, Lorraine V. [7 ]
Lobbestael, Evy [8 ]
Chi, Ruth [1 ]
Ndukwe, Kelechi [1 ]
Ding, Jinhui [2 ]
Nalls, Mike A. [3 ]
Olszewski, Maciej [9 ]
Hauser, David N. [1 ]
Kumaran, Ravindran [1 ]
Lozano, Andres M. [6 ]
Baekelandt, Veerle [8 ]
Greene, Lois E. [9 ]
Taymans, Jean-Marc [8 ]
Greggio, Elisa [4 ]
Cookson, Mark R. [1 ]
机构
[1] NIA, Computat Biol Core, Neurogenet Lab, NIH, Bethesda, MD 20892 USA
[2] NIA, Mol Genet Sect, NIH, Bethesda, MD 20892 USA
[3] Univ Padua, Dept Biol, I-35131 Padua, Italy
[4] Univ Toronto, Univ Hlth Network, Toronto Western Res Inst, Div Brain Imaging & Behav Syst Neurosci, Toronto, ON M5T 2S8, Canada
[5] Univ Toronto, Univ Hlth Network, Toronto Western Res Inst, Dept Surg,Div Neurosurg, Toronto, ON M5T 2S8, Canada
[6] Univ Toronto, Univ Hlth Network, Toronto Western Res Inst, Dept Med,Div Neurosurg, Toronto, ON M5T 2S8, Canada
[7] Katholieke Univ Leuven, Lab Neurobiol & Gene Therapy, B-3000 Louvain, Belgium
[8] NHLBI, Lab Cellular Physiol, NIH, Bethesda, MD 20892 USA
[9] Brown Univ, NIH, Grad Partnership Program, Dept Neurosci, Providence, RI 02912 USA
基金
美国国家卫生研究院;
关键词
BAG5; GAK; trans-Golgi; autophagy; LRRK2; RECRUITMENT; AUTOPHAGY; VARIANTS; CLATHRIN; SEQUENCE; PROTEIN;
D O I
10.1073/pnas.1318306111
中图分类号
O [数理科学和化学]; P [天文学、地球科学]; Q [生物科学]; N [自然科学总论];
学科分类号
07 ; 0710 ; 09 ;
摘要
Mutations in leucine-rich repeat kinase 2 (LRRK2) cause inherited Parkinson disease (PD), and common variants around LRRK2 are a risk factor for sporadic PD. Using protein-protein interaction arrays, we identified BCL2-associated athanogene 5, Rab7L1 (RAB7, member RAS oncogene family-like 1), and Cyclin-G-associated kinase as binding partners of LRRK2. The latter two genes are candidate genes for risk for sporadic PD identified by genome-wide association studies. These proteins form a complex that promotes clearance of Golgi-derived vesicles through the autophagy-lysosome system both in vitro and in vivo. We propose that three different genes for PD have a common biological function. More generally, data integration from multiple unbiased screens can provide insight into human disease mechanisms.
引用
收藏
页码:2626 / 2631
页数:6
相关论文
共 40 条
  • [1] LRRK2 regulates autophagic activity and localizes to specific membrane microdomains in a novel human genomic reporter cellular model
    Alegre-Abarrategui, Javier
    Christian, Helen
    Lufino, Michele M. P.
    Mutihac, Ruxandra
    Venda, Lara Lourenco
    Ansorge, Olaf
    Wade-Martins, Richard
    [J]. HUMAN MOLECULAR GENETICS, 2009, 18 (21) : 4022 - 4034
  • [2] Localization of LRRK2 to membranous and vesicular structures in mammalian brain
    Biskup, Saskia
    Moore, Darren J.
    Celsi, Fulvio
    Higashi, Shinji
    West, Andrew B.
    Andrabi, Shaida A.
    Kurkinen, Kaisa
    Yu, Seong-Woon
    Savitt, Joseph M.
    Waldvogel, Henry J.
    Faull, Richard L. M.
    Emson, Piers C.
    Torp, Reldun
    Ottersen, Ole P.
    Dawson, Ted M.
    Dawson, Valina L.
    [J]. ANNALS OF NEUROLOGY, 2006, 60 (05) : 557 - 569
  • [3] Biochemical Characterization of Highly Purified Leucine-Rich Repeat Kinases 1 and 2 Demonstrates Formation of Homodimers
    Civiero, Laura
    Vancraenenbroeck, Renee
    Belluzzi, Elisa
    Beilina, Alexandra
    Lobbestael, Evy
    Reyniers, Lauran
    Gao, Fangye
    Micetic, Ivan
    De Maeyer, Marc
    Bubacco, Luigi
    Baekelandt, Veerle
    Cookson, Mark R.
    Greggio, Elisa
    Taymans, Jean-Marc
    [J]. PLOS ONE, 2012, 7 (08):
  • [4] The role of leucine-rich repeat kinase 2 (LRRK2) in Parkinson's disease
    Cookson, Mark R.
    [J]. NATURE REVIEWS NEUROSCIENCE, 2010, 11 (12) : 791 - 797
  • [5] Parkinson's disease: insights from pathways
    Cookson, Mark R.
    Bandmann, Oliver
    [J]. HUMAN MOLECULAR GENETICS, 2010, 19 : R21 - R27
  • [6] Sorting nexins provide diversity for retromer-dependent trafficking events
    Cullen, Peter J.
    Korswagen, Hendrik C.
    [J]. NATURE CELL BIOLOGY, 2012, 14 (01) : 29 - 37
  • [7] A comparative study of Lrrk2 function in primary neuronal cultures
    Daechsel, Justus C.
    Behrouz, Bahareh
    Yue, Mei
    Beevers, Joel E.
    Melrose, Heather L.
    Farrer, Matthew J.
    [J]. PARKINSONISM & RELATED DISORDERS, 2010, 16 (10) : 650 - 655
  • [8] Web-Based Genome-Wide Association Study Identifies Two Novel Loci and a Substantial Genetic Component for Parkinson's Disease
    Do, Chuong B.
    Tung, Joyce Y.
    Dorfman, Elizabeth
    Kiefer, Amy K.
    Drabant, Emily M.
    Francke, Uta
    Mountain, Joanna L.
    Goldman, Samuel M.
    Tanner, Caroline M.
    Langston, J. William
    Wojcicki, Anne
    Eriksson, Nicholas
    [J]. PLOS GENETICS, 2011, 7 (06):
  • [9] Inhibition of LRRK2 kinase activity leads to dephosphorylation of Ser910/Ser935, disruption of 14-3-3 binding and altered cytoplasmic localization
    Dzamko, Nicolas
    Deak, Maria
    Hentati, Faycal
    Reith, Alastair D.
    Prescott, Alan R.
    Alessi, Dario R.
    Nichols, R. Jeremy
    [J]. BIOCHEMICAL JOURNAL, 2010, 430 : 405 - 413
  • [10] Leucine-rich repeat kinase 2 regulates autophagy through a calcium-dependent pathway involving NAADP
    Gomez-Suaga, Patricia
    Luzon-Toro, Berta
    Churamani, Dev
    Zhang, Ling
    Bloor-Young, Duncan
    Patel, Sandip
    Woodman, Philip G.
    Churchill, Grant C.
    Hilfiker, Sabine
    [J]. HUMAN MOLECULAR GENETICS, 2012, 21 (03) : 511 - 525