Lessons learned from the Pediatric Cardiomyopathy Registry (PCMR) Study Group

被引:30
作者
Wilkinson, James D. [1 ]
Westphal, Joslyn A. [1 ]
Bansal, Neha [2 ]
Czachor, Jason D. [1 ]
Razoky, Hiedy [1 ]
Lipshultz, Steven E. [1 ,3 ]
机构
[1] Wayne State Univ, Sch Med, Dept Pediat, Childrens Res Ctr Michigan, Detroit, MI 48201 USA
[2] Childrens Hosp Michigan, Dept Pediat, Detroit Med Ctr, Detroit, MI 48201 USA
[3] Univ Miami, Miller Sch Med, Miami, FL 33136 USA
关键词
Cardiomyopathy; paediatrics; patient registry; heart failure; Pediatric Cardiomyopathy Registry; IDIOPATHIC DILATED CARDIOMYOPATHY; ONSET HEART-FAILURE; HYPERTROPHIC CARDIOMYOPATHY; CARDIAC TRANSPLANTATION; CHILDREN; OUTCOMES; EPIDEMIOLOGY; CHILDHOOD; SURVIVAL; DIAGNOSIS;
D O I
10.1017/S1047951115000943
中图分类号
R5 [内科学];
学科分类号
1002 ; 100201 ;
摘要
Cardiomyopathy is a rare disorder of the heart muscle, affecting 1.13 cases per 100,000 children, from birth to 18 years of age. Cardiomyopathy is the leading cause of heart transplantation in children over the age of 1. The Pediatric Cardiomyopathy Registry funded in 1994 by the National Heart, Lung, and Blood Institute was established to examine the epidemiology of the disease in children below 18 years of age. More than 3500 children across the United States and Canada have been enrolled in the Pediatric Cardiomyopathy Registry, which has followed-up these patients until death, heart transplantation, or loss to follow-up. The Pediatric Cardiomyopathy Registry has provided the most in-depth illustration of this disease regarding its aetiology, clinical course, associated risk factors, and patient outcomes. Data from the registry have helped in guiding the clinical management of cardiomyopathy in children under 18 years of age; however, questions still remain regarding the most clinically effective diagnostic and treatment approaches for these patients. Future directions of the registry include the use of next-generation whole-exome sequencing and cardiac biomarkers to identify aetiology-specific treatments and improve diagnostic strategies. This article provides a brief synopsis of the work carried out by the Pediatric Cardiomyopathy Registry since its inception, including the current knowledge on the aetiologies, outcomes, and treatments of cardiomyopathy in children.
引用
收藏
页码:140 / 153
页数:14
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