Management of lipoprotein X and its complications in a patient with primary sclerosing cholangitis

被引:18
作者
Brandt, Eric J. [1 ]
Regnier, Shane M. [2 ]
Leung, Edward K. Y. [2 ,3 ]
Chou, Sharon H. [1 ,4 ]
Baron, Beverly W. [2 ,3 ]
Te, Helen S. [2 ,5 ]
Davidson, Michael H. [2 ,6 ]
Sargis, Robert M. [1 ,2 ,4 ]
机构
[1] Univ Chicago, Dept Med, Chicago, IL 60637 USA
[2] Univ Chicago, Pritzker Sch Med, Chicago, IL 60637 USA
[3] Univ Chicago, Dept Pathol, Chicago, IL 60637 USA
[4] Univ Chicago, Sect Endocrinol Diabet & Metab, Chicago, IL 60637 USA
[5] Univ Chicago, Sect Gastroenterol, Chicago, IL 60637 USA
[6] Univ Chicago, Sect Cardiol, Chicago, IL 60637 USA
关键词
cholestasis; hypercholesterolemia; lipoprotein X; neuropathy; plasma exchange; primary sclerosing cholangitis; statin; xanthoma; PRIMARY BILIARY-CIRRHOSIS; CHARACTERIZING OBSTRUCTIVE-JAUNDICE; CHOLESTEROL-METABOLISM; URSODEOXYCHOLIC ACID; FAMILIAL LECITHIN; LCAT DEFICIENCY; CHOLESTASIS; PLASMA; IDENTIFICATION; SIMVASTATIN;
D O I
10.2217/clp.15.23
中图分类号
Q5 [生物化学]; Q7 [分子生物学];
学科分类号
071010 ; 081704 ;
摘要
Lipoprotein X (LpX) is an abnormal lipoprotein found in conditions such as lecithin:cholesterol acyltransferase deficiency and cholestatic states (e.g., primary biliary cirrhosis and primary sclerosing cholangitis). Management of severe hypercholesterolemia due to LpX with drugs and physical removal methods is not well established in the literature. A case is discussed of a 51-year-old woman who presented with multiple electrolyte abnormalities, xanthomas and neuropathy found to be secondary to LpX in the setting of primary sclerosing cholangitis. This case highlights that oral medications, including statins, may be insufficient to normalize lipid levels or improve clinical symptoms of LpX and presents therapeutic plasma exchange as a safe and effective therapeutic option to treat the morbid sequela of LpX hyperlipidemia.
引用
收藏
页码:305 / 312
页数:8
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