Functional basic reading skills in Williams syndrome

被引:5
作者
Brawn, Gabrielle [1 ]
Kohnen, Saskia [1 ,2 ]
Tassabehji, May [3 ]
Porter, Melanie [1 ,2 ]
机构
[1] Macquarie Univ, Dept Psychol, Sydney, NSW 2109, Australia
[2] Macquarie Univ, Ctr Atyp Neurodev, Sydney, NSW, Australia
[3] Univ Manchester, Med Genet, Manchester, Lancs, England
关键词
PHONOLOGICAL AWARENESS; COGNITIVE-ABILITIES; DEVELOPMENTAL TRAJECTORIES; INTELLECTUAL DISABILITIES; METHODOLOGICAL ISSUES; BEUREN-SYNDROME; DOWN-SYNDROME; CHILDREN; PHENOTYPE; DYSLEXIA;
D O I
10.1080/87565641.2018.1455838
中图分类号
B844 [发展心理学(人类心理学)];
学科分类号
040202 ;
摘要
This study investigated whether individuals with Williams syndrome (WS) can attain a functional level of basic reading skills. The Study also investigated broader cognitive factors associated with reading ability in individuals with WS. Thirty individuals with WS participated in this study (mean chronological age 21years and mean mental age 7years 7months). The results supported our hypotheses that: firstly, reading abilities would be heterogeneous in WS; secondly, at least some WS individuals are capable of achieving a functional basic reading level; and thirdly, on average, WS individuals would find reading of nonwords more difficult than reading of regular and irregular words. Moreover, higher reading ability was found to be associated with increased outcomes in adaptive functioning, in particular, Written and Expressive Communication skills and Community Living skills, highlighting the potential benefits of developing reading abilities in WS. Although Intelligence Quotient (IQ) was related to overall basic reading ability generally, it was not found to be a determining factor in reading subtypes. Several cognitive skills known to be related to reading ability in typically developing individuals were found to be associated with reading performance and reading subtypes. Implications for appropriate reading instruction are discussed.
引用
收藏
页码:454 / 477
页数:24
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