Clinical significance of clonality assessment in JAK2V617F-negative essential thrombocythemia

被引:7
作者
Martinez-Aviles, Luz [2 ,3 ]
Alvarez-Larran, Alberto [1 ,3 ]
Besses, Carles [1 ]
Navarro, Gemma [2 ]
Torres, Erica [2 ]
Longaron, Raquel [2 ]
Angona, Anna [1 ]
Pedro, Carme [1 ]
Florensa, Lourdes [2 ]
Serrano, Sergi [2 ,3 ]
Bellosillo, Beatriz [2 ,4 ]
机构
[1] Hosp del Mar, Dept Clin Hematol, IMIM, Barcelona 08003, Spain
[2] Hosp del Mar, Dept Pathol, IMIM, Barcelona 08003, Spain
[3] Univ Autonoma Barcelona, E-08193 Barcelona, Spain
[4] Univ Pompeu Fabra, Barcelona, Spain
关键词
Clonality; Essential thrombocythemia; Disease transformation; TYROSINE KINASE JAK2; POLYCYTHEMIA-VERA; ASXL1; GENE; MUTATION; TET2; DISORDERS;
D O I
10.1007/s00277-012-1502-6
中图分类号
R5 [内科学];
学科分类号
1002 ; 100201 ;
摘要
JAK2V617F-negative essential thrombocythemia (ET) is a heterogeneous disease including clonal cases and others without evidence of clonality. However, it is unknown if the detection of myeloid clonality in JAK2V617F-negative ET patients confers a different clinical outcome than those in whom clonal hematopoiesis cannot be demonstrated. The objective of the present study was to evaluate the clinical significance of clonality assessment in patients with JAK2V617F-negative ET. Clonality investigation including mutational status of MPL, TET2, and ASXL1 genes and human androgen receptor (HUMARA) assay was performed in 73 JAK2V617F-negative cases out of 186 subjects consecutively diagnosed with ET in a single institution, at diagnosis or during follow-up. Mutations in MPL, TET2, and ASXL1 were observed in 7, 4, and 2 cases, respectively, whereas clonality by HUMARA assay was demonstrated in 21 out of 46 (46 %) female patients. With a median follow-up of 8 years, death, thrombosis, bleeding, and disease transformation were registered in 7, 10, 8, and 6 patients, respectively. No differences in thrombosis, bleeding or survival were observed according to clonality assessment. The probability of disease transformation at 10 years was higher in patients showing clonal hematopoiesis by presenting mutations in either MPL, TET2, or ASXL1 (64 versus 2 % in patients without mutations, p < 0.001) and in those with HUMARA clonality (35 versus 0 % in patients with polyclonal hematopoiesis, p < 0.004). In conclusion, disease transformation is associated with evidence of clonality in JAK2V617F-negative ET.
引用
收藏
页码:1555 / 1562
页数:8
相关论文
共 22 条
[1]   Genetics of the myeloproliferative neoplasms [J].
Abdel-Wahab, Omar .
CURRENT OPINION IN HEMATOLOGY, 2011, 18 (02) :117-123
[2]   Genetic characterization of TET1, TET2, and TET3 alterations in myeloid malignancies [J].
Abdel-Wahab, Omar ;
Mullally, Ann ;
Hedvat, Cyrus ;
Garcia-Manero, Guillermo ;
Patel, Jay ;
Wadleigh, Martha ;
Malinge, Sebastien ;
Yao, JinJuan ;
Kilpivaara, Outi ;
Bhat, Rukhmi ;
Huberman, Kety ;
Thomas, Sabrena ;
Dolgalev, Igor ;
Heguy, Adriana ;
Paietta, Elisabeth ;
Le Beau, Michelle M. ;
Beran, Miloslav ;
Tallman, Martin S. ;
Ebert, Benjamin L. ;
Kantarjian, Hagop M. ;
Stone, Richard M. ;
Gilliland, D. Gary ;
Crispino, John D. ;
Levine, Ross L. .
BLOOD, 2009, 114 (01) :144-147
[3]   Clinical implications of the JAK2 V617F mutation in essential thrombocythemia [J].
Antonioli, E ;
Guglielmelli, P ;
Pancrazzi, A ;
Bogani, C ;
Verrucci, M ;
Ponziani, V ;
Longo, G ;
Bosi, A ;
Vannucchi, AM .
LEUKEMIA, 2005, 19 (10) :1847-1849
[4]   Response criteria for essential thrombocythemia and polycythemia vera: result of a European LeukemiaNet consensus conference [J].
Barosi, Giovanni ;
Birgegard, Gunnar ;
Finazzi, Guido ;
Griesshammer, Martin ;
Harrison, Claire ;
Hasselbalch, Hans Carl ;
Kiladjian, Jean-Jacques ;
Lengfelder, Eva ;
McMullin, Mary Frances ;
Passamonti, Francesco ;
Reilly, John T. ;
Vannucchi, Alessandro M. ;
Barbui, Tiziano .
BLOOD, 2009, 113 (20) :4829-4833
[5]   Acquired mutation of the tyrosine kinase JAK2 in human myeloproliferative disorders [J].
Baxter, EJ ;
Scott, LM ;
Campbell, PJ ;
East, C ;
Fourouclas, N ;
Swanton, S ;
Vassiliou, GS ;
Bench, AJ ;
Boyd, EM ;
Curtin, N ;
Scott, MA ;
Erber, WN ;
Green, AR .
LANCET, 2005, 365 (9464) :1054-1061
[6]   MPL mutations in myeloproliferative disorders:: analysis of the PT-1 cohort [J].
Beer, Philip A. ;
Campbell, Peter J. ;
Scott, Linda M. ;
Bench, Anthony J. ;
Erber, Wendy N. ;
Bareford, David ;
Wilkins, Bridget S. ;
Reilly, John T. ;
Hasselbalch, Hans C. ;
Bowman, Richard ;
Wheatley, Keith ;
Buck, Georgina ;
Harrison, Claire N. ;
Green, Anthony R. .
BLOOD, 2008, 112 (01) :141-149
[7]   Clinical utility of routine MPL exon 10 analysis in the diagnosis of essential thrombocythaemia and primary myelofibrosis [J].
Boyd, Elaine M. ;
Bench, Anthony J. ;
Goday-Fernandez, Andrea ;
Anand, Shubha ;
Vaghela, Krishna J. ;
Beer, Phillip ;
Scott, Mike A. ;
Bareford, David ;
Green, Anthony R. ;
Huntly, Brian ;
Erber, Wendy N. .
BRITISH JOURNAL OF HAEMATOLOGY, 2010, 149 (02) :250-257
[8]   Mutations of ASXL1 gene in myeloproliferative neoplasms [J].
Carbuccia, N. ;
Murati, A. ;
Trouplin, V. ;
Brecqueville, M. ;
Adelaide, J. ;
Rey, J. ;
Vainchenker, W. ;
Bernard, O. A. ;
Chaffanet, M. ;
Vey, N. ;
Birnbaum, D. ;
Mozziconacci, M. J. .
LEUKEMIA, 2009, 23 (11) :2183-2186
[9]   Mutation in TET2 in Myeloid Cancers [J].
Delhommeau, Francois ;
Dupont, Sabrina ;
Della Valle, Veronique ;
James, Chloe ;
Trannoy, Severine ;
Masse, Aline ;
Kosmider, Olivier ;
Le Couedic, Jean-Pierre ;
Robert, Fabienne ;
Alberdi, Antonio ;
Lecluse, Yann ;
Plo, Isabelle ;
Dreyfus, Francois J. ;
Marzac, Christophe ;
Casadevall, Nicole ;
Lacombe, Catherine ;
Romana, Serge P. ;
Dessen, Philippe ;
Soulier, Jean ;
Viguie, Franck ;
Fontenay, Michaela ;
Vainchenker, William ;
Bernard, Olivier A. .
NEW ENGLAND JOURNAL OF MEDICINE, 2009, 360 (22) :2289-2301
[10]   Hereditary thrombocythaemia in a Japanese family is caused by a novel point mutation in the thrombopoietin gene [J].
Ghilardi, N ;
Wiestner, A ;
Kikuchi, M ;
Ohsaka, A ;
Skoda, RC .
BRITISH JOURNAL OF HAEMATOLOGY, 1999, 107 (02) :310-316