An Investigation of Narrative Ability in Boys with Autism and Fragile X Syndrome

被引：38

作者：

Hogan-Brown, Abigail L. ^{[1
]}

Losh, Molly ^{[2
]}

Martin, Gary E. ^{[3
]}

Mueffelmann, Deborah J. ^{[3
]}

机构：

[1] Northwestern Univ, Evanston, IL 60208 USA

[2] Northwestern Univ, Roxelyn & Richard Pepper Dept Commun Sci & Disord, Evanston, IL 60208 USA

[3] Univ N Carolina, Frank Porter Graham Child Dev Inst, Chapel Hill, NC USA

来源：

AJIDD-AMERICAN JOURNAL ON INTELLECTUAL AND DEVELOPMENTAL DISABILITIES | 2013年 / 118卷 / 02期

关键词：

autism; Fragile X syndrome; narrative; mental age; FMR1; Down syndrome; DIAGNOSTIC OBSERVATION SCHEDULE; MENTAL-RETARDATION PROTEIN; HIGH-FUNCTIONING CHILDREN; SEX-DIFFERENCES; EXPRESSIVE LANGUAGE; YOUNG-ADULTS; DOWN-SYNDROME; CONVERSATIONAL CHARACTERISTICS; SPECTRUM DISORDER; ADOLESCENTS;

D O I：

10.1352/1944-7558-118.2.77

中图分类号：

G76 [特殊教育];

学科分类号：

040109 ;

摘要：

Whereas pragmatic language difficulties are characteristic of both autism and Fragile X syndrome, it is unclear whether such deficits are qualitatively similar or whether certain skills are differentially affected. This study compared narrative competence in boys with autism, Fragile X syndrome, Down syndrome, and typical development. Results revealed that an interaction between diagnosis and nonverbal mental age predicted narrative microstructure (e. g., complex syntax) but not macrostructure (e. g., thematic maintenance). Correlations with FMR1-related variation were investigated in children with Fragile X syndrome. While CGG repeat length was associated with many language characteristics, nonverbal IQ appeared to mediate these relationships. These findings are an important step toward understanding narrative abilities in boys with and without the FMR1 mutation.

引用

页码：77 / 94

页数：18

共 113 条

[61]

Labov W., 1967, STUDY NONSTANDARD EN, P286

[62] THE EFFECT OF SOCIAL-CONTEXT ON THE FUNCTIONAL COMMUNICATION-SKILLS OF AUTISTIC-CHILDREN [J].