Polymorphisms in the Human Tropoelastin Gene Modify In Vitro Self-Assembly and Mechanical Properties of Elastin-Like Polypeptides

被引:19
作者
He, David [1 ,2 ]
Miao, Ming [1 ]
Sitarz, Eva E. [1 ]
Muiznieks, Lisa D. [1 ]
Reichheld, Sean [1 ]
Stahl, Richard J. [1 ]
Keeley, Fred W. [1 ,3 ]
Parkinson, John [1 ,2 ,3 ]
机构
[1] Hosp Sick Children, Program Mol Struct & Funct, Toronto, ON M5G 1X8, Canada
[2] Univ Toronto, Dept Mol Genet, Toronto, ON, Canada
[3] Univ Toronto, Dept Biochem, Toronto, ON, Canada
来源
PLOS ONE | 2012年 / 7卷 / 09期
基金
加拿大健康研究院;
关键词
SEQUENCE; PROTEIN; ASSOCIATION; DISSECTION; DOMAIN; COACERVATION; DETERMINANTS; AGGREGATION; MORPHOLOGY; ANEURYSMS;
D O I
10.1371/journal.pone.0046130
中图分类号
O [数理科学和化学]; P [天文学、地球科学]; Q [生物科学]; N [自然科学总论];
学科分类号
07 ; 0710 ; 09 ;
摘要
Elastin is a major structural component of elastic fibres that provide properties of stretch and recoil to tissues such as arteries, lung and skin. Remarkably, after initial deposition of elastin there is normally no subsequent turnover of this protein over the course of a lifetime. Consequently, elastic fibres must be extremely durable, able to withstand, for example in the human thoracic aorta, billions of cycles of stretch and recoil without mechanical failure. Major defects in the elastin gene (ELN) are associated with a number of disorders including Supravalvular aortic stenosis (SVAS), Williams-Beuren syndrome (WBS) and autosomal dominant cutis laxa (ADCL). Given the low turnover of elastin and the requirement for the long term durability of elastic fibres, we examined the possibility for more subtle polymorphisms in the human elastin gene to impact the assembly and long-term durability of the elastic matrix. Surveys of genetic variation resources identified 118 mutations in human ELN, 17 being non-synonymous. Introduction of two of these variants, G422S and K463R, in elastin-like polypeptides as well as full-length tropoelastin, resulted in changes in both their assembly and mechanical properties. Most notably G422S, which occurs in up to 40% of European populations, was found to enhance some elastomeric properties. These studies reveal that even apparently minor polymorphisms in human ELN can impact the assembly and mechanical properties of the elastic matrix, effects that over the course of a lifetime could result in altered susceptibility to cardiovascular disease.
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页数:12
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