A rare case of acquired hemophilia A associated with myelodysplastic syndrome

被引:0
作者
Raval, Mihir [1 ,2 ,3 ]
Kallamadi, Rekha [1 ,2 ,3 ]
Bande, Dinesh [1 ,2 ,3 ]
机构
[1] Sanford Hosp, Dept Internal Med, Fargo, ND USA
[2] Univ N Dakota, Sch Med, Grand Forks, ND 58202 USA
[3] Sanford Hlth, Roger Maris Canc Ctr, Fargo, ND USA
关键词
Factor VIII; acquired hemophilia A; rFVIIa; bethesda assay; myelodysplastic syndrome; aPTT; factor VIII inhibitor; FACTOR-VIII INHIBITOR;
D O I
暂无
中图分类号
R-3 [医学研究方法]; R3 [基础医学];
学科分类号
1001 ;
摘要
84 year old male with past medical history of myelodysplastic syndrome (MDS) presented with progressive subcutaneous and muscle bleed in the right forearm and arm. Workup revealed elevated activated partial thromboplastin time (aPTT) - 71.8 seconds (normal 23 - 32 seconds) which was persistently elevated after mixing study (37.1 seconds immediately and 51.1 seconds after 1 hour). Further laboratory work up revealed low factor VIII level (3%) and elevated factor VIII inhibitor by Bethesda assay (3 units/ml of blood). Acquired hemophilia A (AHA) diagnosis was established and patient was treated with recombinant factor VIIa (rFVlla) to control the bleeding and also prednisone for immunosuppression. Subsequent monitoring suggested reduction of factor VIII inhibitor - antibody levels to undetectable level in 3 days and increase of factor VIII level from 3% to 50% in 5 days. Despite of improvement in the laboratory values he continued to have progression of his bleeding which involved posterior chest wall and also left arm. Due to the progression of the condition and prior expressed wish family decided to stop the aggressive treatment and patient died nine days after the diagnosis. The case report describes a rare presentation of AHA in MDS (With bone marrow cytogenetics abnormality) patient with fatal outcome.
引用
收藏
页码:262 / 266
页数:5
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