Two-Stage TMLE to reduce bias and improve efficiency in cluster randomized trials

被引:21
作者
Balzer, Laura B. [1 ]
van der Laan, Mark [2 ]
Ayieko, James [3 ]
Kamya, Moses [4 ,5 ]
Chamie, Gabriel [6 ]
Schwab, Joshua [2 ]
Havlir, Diane, V [6 ]
Petersen, Maya L. [2 ]
机构
[1] Univ Massachusetts, Dept Biostat & Epidemiol, 715 North Pleasant St, Amherst, MA 01003 USA
[2] Univ Calif Berkeley, Div Biostat, 2121 Berkeley Way, Berkeley, CA 94720 USA
[3] Kenya Govt Med Res Ctr, Ctr Microbiol Res, POB 54840 00200 Off Raila Odinga Way, Nairobi, Kenya
[4] Makerere Univ, Dept Med, POB 7475, Kampala, Uganda
[5] Infect Dis Res Collaborat, POB 7475, Kampala, Uganda
[6] Univ Calif San Francisco, Dept Med, 995 Potrero Ave, San Francisco, CA 94143 USA
基金
美国国家卫生研究院;
关键词
Clustered data; Cluster randomized trials; Covariate adjustment; Data-adaptive; Double robust; Group randomized trials; Missing data; Multi-level models; Super Learner; TMLE; RECENT METHODOLOGICAL DEVELOPMENTS; COVARIATE-DEPENDENT MISSINGNESS; CAUSAL INFERENCE; BINARY OUTCOMES; MODELS; DESIGN; LEVEL;
D O I
10.1093/biostatistics/kxab043
中图分类号
Q [生物科学];
学科分类号
07 ; 0710 ; 09 ;
摘要
Cluster randomized trials (CRTs) randomly assign an intervention to groups of individuals (e.g., clinics or communities) and measure outcomes on individuals in those groups. While offering many advantages, this experimental design introduces challenges that are only partially addressed by existing analytic approaches. First, outcomes are often missing for some individuals within clusters. Failing to appropriately adjust for differential outcome measurement can result in biased estimates and inference. Second, CRTs often randomize limited numbers of clusters, resulting in chance imbalances on baseline outcome predictors between arms. Failing to adaptively adjust for these imbalances and other predictive covariates can result in efficiency losses. To address these methodological gaps, we propose and evaluate a novel two-stage targeted minimum loss-based estimator to adjust for baseline covariates in a manner that optimizes precision, after controlling for baseline and postbaseline causes of missing outcomes. Finite sample simulations illustrate that our approach can nearly eliminate bias due to differential outcome measurement, while existing CRT estimators yield misleading results and inferences. Application to real data from the SEARCH community randomized trial demonstrates the gains in efficiency afforded through adaptive adjustment for baseline covariates, after controlling for missingness on individual-level outcomes.
引用
收藏
页码:502 / 517
页数:16
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