Insights into elastic fiber fragmentation: Mechanisms and treatment of aortic aneurysm in Marfan syndrome

被引:6
|
作者
Seeburun, Sheilabi [1 ,4 ,5 ]
Wu, Shichao [1 ]
Hemani, Darshi [2 ]
Pham, Lucynda [1 ,2 ]
Ju, Donghong [1 ,3 ]
Xie, Youming [3 ]
Kata, Priyaranjan [1 ]
Li, Li [1 ,2 ,4 ]
机构
[1] Wayne State Univ, Dept Internal Med, Detroit, MI USA
[2] Wayne State Univ, Ctr Mol Med & Genet, Detroit, MI USA
[3] Wayne State Univ, Dept Oncol, Detroit, MI USA
[4] 421 E Canfield Ave,Room 2146, Detroit, MI 48201 USA
[5] Rutgers Hlth Community Med Ctr, Dept Internal Med, Toms River, NJ USA
关键词
Elastic fiber fragmentation; Marfan syndrome; Fibrillin-1; Aortic aneurysm; MMP; TGF-beta; Elastin; Losartan; Angiotensin receptor blocker (ARB); SMOOTH-MUSCLE-CELLS; TGF-BETA; MOUSE MODEL; FIBRILLIN; BINDING; PATHOGENESIS; EXPRESSION; LOSARTAN; MICROFIBRILS; PROGRESSION;
D O I
10.1016/j.vph.2023.107215
中图分类号
R9 [药学];
学科分类号
1007 ;
摘要
Marfan syndrome (MFS) is an autosomal dominant connective tissue disorder caused by mutations in fibrillin 1 (FBN1) gene. These mutations result in defects in the skeletal, ocular, and cardiovascular systems. Aortic aneurysm is the leading cause of premature mortality in untreated MFS patients. Elastic fiber fragmentation in the aortic vessel wall is a hallmark of MFS-associated aortic aneurysms. FBN1 mutations result in FBN1 fragments that also contribute to elastic fiber fragmentation. Although recent research has advanced our understanding of MFS, the contribution of elastic fiber fragmentation to the pathogenesis of aneurysm formation remains poorly understood. This review provides a comprehensive overview of the molecular mechanisms of elastic fiber fragmentation and its role in the pathogenesis of aortic aneurysm progression. Increased comprehension of elastic fragmentation has significant clinical implications for developing targeted interventions to block aneurysm progression, which would benefit not only individuals with Marfan syndrome but also other patients with aneurysms. Moreover, this review highlights an overlooked connection between inhibiting aneurysm and the restoration of elastic fibers in the vessel wall with various aneurysm inhibitors, including drugs and chemicals. Investigating the underlying molecular mechanisms could uncover innovative therapeutic strategies to inhibit elastin fragmentation and prevent the progression of aneurysms.
引用
收藏
页数:8
相关论文
共 50 条
  • [31] LUMBOSACRAL MENINGOCELE AND AORTIC-ANEURYSM IN MARFAN-SYNDROME
    ARROVO, JF
    GARCIA, JF
    SKELETAL RADIOLOGY, 1989, 18 (08) : 614 - 618
  • [32] Results of surgery for aortic root aneurysm in patients with Marfan syndrome
    de Oliveira, NC
    David, TE
    Ivanov, J
    Armstrong, S
    Eriksson, MJ
    Rakowski, H
    Webb, G
    JOURNAL OF THORACIC AND CARDIOVASCULAR SURGERY, 2003, 125 (04): : 789 - 796
  • [33] Abdominal Aortic Aneurysm in Marfan Syndrome: Time for Screening Guidelines?
    Hagerty, Tracy
    Geraghty, Patrick
    Braverman, Alan C.
    CIRCULATION, 2015, 132
  • [34] Current status of thoracoabdominal aortic aneurysm repair in Marfan syndrome
    Coselli, JS
    LeMaire, SA
    JOURNAL OF CARDIAC SURGERY, 1997, 12 (02) : 167 - 172
  • [35] EMMPRIN is involved in thoracic aortic aneurysm of Marfan syndrome patients
    Perrucci, G. L.
    Rurali, E.
    Piccoli, M.
    Pini, A.
    Antona, C.
    Egea, G.
    Polvani, G.
    Alamanni, F.
    Nigro, P.
    Pompilio, G.
    EUROPEAN HEART JOURNAL, 2018, 39 : 929 - 929
  • [36] Pregnancy Risk in Marfan Syndrome: The Cornell Aortic Aneurysm Registry
    Narula, Nupoor
    Devereux, Richard B.
    Malonga, Grace
    Hriljac, Ingrid
    Roman, Mary J.
    CIRCULATION, 2018, 138
  • [37] Marfan syndrome presenting with abdominal aortic aneurysm during pregnancy
    Pasternak, J.
    Kacanski, M.
    Budakov, N.
    EUROPEAN SURGERY-ACTA CHIRURGICA AUSTRIACA, 2017, 49 (01): : 38 - 40
  • [38] Monozygotic twins with Marfan's syndrome and ascending aortic aneurysm
    Redruello, Hector Jorge
    Cianciulli, Tomas Francisco
    Rostello, Eduardo Fernandez
    Recalde, Barbara
    Lax, Jorge Alberto
    Picone, Victorio Prospero
    Belforte, Sandro Mario
    Prezioso, Horacio Alberto
    EUROPEAN JOURNAL OF ECHOCARDIOGRAPHY, 2007, 8 (04): : 302 - 306
  • [39] Therapy Insight: aortic aneurysm and dissection in Marfan's syndrome
    Francesco Ramirez
    Harry C Dietz
    Nature Clinical Practice Cardiovascular Medicine, 2004, 1 : 31 - 36
  • [40] Therapy insight: aortic aneurysm and dissection in Marfan's syndrome
    Ramirez, Francesco
    Dietz, Harry C.
    NATURE CLINICAL PRACTICE CARDIOVASCULAR MEDICINE, 2004, 1 (01): : 31 - 36