Molecular basis of retinal remodeling in a zebrafish model of retinitis pigmentosa

被引:9
作者
Santhanam, Abirami [1 ,2 ,5 ]
Shihabeddin, Eyad [1 ,3 ]
Wei, Haichao [4 ]
Wu, Jiaqian [3 ,4 ]
O'Brien, John [1 ,2 ,3 ]
机构
[1] Univ Texas Hlth Sci Ctr Houston, McGovern Med Sch, Dept Ophthalmol & Visual Sci, Houston, TX 77030 USA
[2] Univ Houston Coll Optometry, Coll Optometry, Houston, TX 77204 USA
[3] MD Anderson UT Hlth Grad Sch Biomed Sci, Houston, TX 77030 USA
[4] Univ Texas Hlth Sci Ctr Houston, McGovern Med Sch, Dept Neurosurg, Houston, TX 77030 USA
[5] Baylor Coll Med, Human Genome Sequencing Ctr, Houston, TX 77030 USA
关键词
Retinitis pigmentosa; Retinal degeneration; Regeneration; Photoreceptor; Pigmented epithelium; Synapse remodeling; Oxidative metabolism; MOUSE MODEL; CELL-DEATH; ROD DEGENERATION; CONE SURVIVAL; GENE-THERAPY; PROTEIN; EXPRESSION; BIPOLAR; COMPLEX; CLOCK;
D O I
10.1007/s00018-023-05021-1
中图分类号
Q5 [生物化学]; Q7 [分子生物学];
学科分类号
071010 ; 081704 ;
摘要
A hallmark of inherited retinal degenerative diseases such as retinitis pigmentosa (RP) is progressive structural and functional remodeling of the remaining retinal cells as photoreceptors degenerate. Extensive remodeling of the retina stands as a barrier for the successful implementation of strategies to restore vision. To understand the molecular basis of remodeling, we performed analyses of single-cell transcriptome data from adult zebrafish retina of wild type AB strain (WT) and a P23H mutant rhodopsin transgenic model of RP with continuous degeneration and regeneration. Retinas from both female and male fish were pooled to generate each library, combining data from both sexes. We provide a benchmark atlas of retinal cell type transcriptomes in zebrafish and insight into how each retinal cell type is affected in the P23H model. Oxidative stress is found throughout the retina, with increases in reliance on oxidative metabolism and glycolysis in the affected rods as well as cones, bipolar cells, and retinal ganglion cells. There is also transcriptional evidence for widespread synaptic remodeling and enhancement of glutamatergic transmission in the inner retina. Notably, changes in circadian rhythm regulation are detected in cones, bipolar cells, and retinal pigmented epithelium. We also identify the transcriptomic signatures of retinal progenitor cells and newly formed rods essential for the regenerative process. This comprehensive transcriptomic analysis provides a molecular road map to understand how the retina remodels in the context of chronic retinal degeneration with ongoing regeneration.
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页数:24
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