Revelation of Rapunzel syndrome: A rare case report of gastric trichobezoar-induced acute purulent peritonitis

被引:0
作者
Belhadj, Anis
Touati, Med Dheker
Ben Othmane, Mohamed Raouf
Khefacha, Fahd
Saidani, Ahmed
Chebbi, Faouzi
机构
[1] Mahmoud El Matri Hosp, Gen Surg Dept, V59M 628, Ariana, Tunisia
[2] Univ Tunis El Manar, Fac Med Tunis, Rue Fac Med,R534 F9H, Tunis, Tunisia
来源
INTERNATIONAL JOURNAL OF SURGERY CASE REPORTS | 2023年 / 111卷
关键词
Trichobezoar; Gastric perforation; Acute peritonitis; Surgical intervention; Rapunzel syndrome; Trichophagia; INTUSSUSCEPTION;
D O I
10.1016/j.ijscr.2023.108860
中图分类号
R61 [外科手术学];
学科分类号
摘要
Introduction and importance: The Rapunzel syndrome embodies an uncommon variation of trichobezoar, pre-dominantly observed among individuals with a history of psychiatric conditions, trichotillomania, and tricho-phagia. This combination of factors predisposes to the eventual formation of gastric bezoars. Trichobezoars, infrequent gastric masses composed of hair, can lead to complications if left untreated.Case report: A 19-year-old female hairdresser with a history of trichophagia sought medical attention due to abdominal pain and episodes of vomiting. With an elevated body temperature and abdominal rigidity, imaging revealed the presence of a trichobezoar, accompanied by pneumoperitoneum and intraperitoneal effusion. Ur-gent surgical intervention confirmed the diagnosis of generalized purulent acute peritonitis, triggered by a gastric perforation caused by a 20 cm trichobezoar with an extension into the duodenum, which defines the Rapunzel syndrome. Gastrotomy was performed to remove the trichobezoar, followed by thorough peritoneal lavage.Clinical discussion: Trichobezoar is a rare condition that involves the abnormal accumulation of solid substances, particularly hair, within the stomach. Known as "Rapunzel syndrome," it can extend into the duodenum or jejunum. Commonly associated with emotional disorders, trichobezoar can lead to symptoms like epigastric discomfort, vomiting, and weight loss. Diagnosis is through endoscopy, and treatments include fluid intake, endoscopic extraction, chemical dissolution, and surgical removal. Surgical intervention is often preferred, with laparoscopic approaches considered. Psychiatric management is often required for patients.Conclusion: This case underscores the uncommon Rapunzel syndrome presentation, emphasizing timely surgical measures and multidisciplinary care for trichobezoars causing acute peritonitis.
引用
收藏
页数:4
相关论文
共 32 条
  • [21] The Rapunzel syndrome (trichohezoar) causing gastric perforation in a child: A case report
    Pul, N
    Pul, M
    EUROPEAN JOURNAL OF PEDIATRICS, 1996, 155 (01) : 18 - 19
  • [22] A rare giant gastric trichobezoar in a young female patient: Case report and review of the literature
    Delimpaltadaki, Dimitra G.
    Gkionis, Ioannis G.
    Flamourakis, Mathaios E.
    Strehle, Andreas F.
    Bachlitzanakis, Emmanouil N.
    Giakoumakis, Michail, I
    Christodoulakis, Manousos S.
    Spiridakis, Konstantinos G.
    CLINICAL CASE REPORTS, 2021, 9 (12):
  • [23] Rapunzel Syndrome A Rare Case Requiring Surgical Management of Acute Pancreatitis
    Winsett, Frank
    Ting, Jose
    Harting, Matthew T.
    PANCREAS, 2019, 48 (05) : E38 - E39
  • [24] Rapunzel syndrome in adult with mysterious presentation: a rare case report with literature review
    Kumar, Navin
    Huda, Farhanul
    Gupta, Rohit
    Payal, Y. S.
    Kumar, Utkarsh
    Mallik, Dhiraj
    TROPICAL DOCTOR, 2019, 49 (02) : 133 - 135
  • [25] Mallory-Weiss syndrome from giant gastric trichobezoar: A case report
    Lieto, Eva
    Auricchio, Annamaria
    Belfiore, Maria Paola
    Del Sorbo, Giovanni
    De Sena, Gabriele
    Napolitano, Vincenzo
    Ruggiero, Alessio
    Galizia, Gennaro
    Cardella, Francesca
    WORLD JOURNAL OF GASTROINTESTINAL SURGERY, 2023, 15 (05): : 972 - 977
  • [26] Acute Case of Trichobezoar Diagnosed From Computed Tomography and 3D Images: Rapunzel Syndrome Re-examined
    Kyin, Cynthia
    Patel, Pushpak
    Casas-Melley, Adela
    Abdalla, Wael M.
    Westmoreland, Tamarah
    CUREUS JOURNAL OF MEDICAL SCIENCE, 2023, 15 (02)
  • [27] Gastric Large-Cell Neuroendocrine Carcinoma Presenting as Perforation Peritonitis: a Rare Case Report
    Ramnath Aishwarya
    Ankit Jain
    Souradeep Dutta
    Reddy Abhinaya
    Pampa Ch Toi
    Vishnu Prasad Nelamangala Ramakrishnaiah
    SN Comprehensive Clinical Medicine, 5 (1)
  • [28] Perforated degenerated immature teratoma of the ovary: Rare cause of acute peritonitis, case report and review of the literature
    Ayoub, Madani
    Touihar, Salma
    Ouazni, Mohamed
    Sanae, Abbaoui
    Hicham, Nassik
    Soufi, Mehdi
    INTERNATIONAL JOURNAL OF SURGERY CASE REPORTS, 2024, 121
  • [29] Rapunzel syndrome associated with trichotillomania and pica causing bowel obstruction in a 4 year-old-female: A rare case report from Nepal
    Pokhrel, Milan
    Yadav, Kundan Kumar
    Khadka, Rabi
    Verma, Rupesh
    Koirala, Dinesh
    Dahal, Geha Raj
    INTERNATIONAL JOURNAL OF SURGERY CASE REPORTS, 2025, 126
  • [30] PEUTZ JEGHERS SYNDROME PRESENTING WITH ACUTE INTESTINAL OBSTRUCTION: A RARE CASE REPORT WITH REVIEW OF LITERATURES
    Hota, P. K.
    Reddy, G. Narasimha
    Rajasekhar, G.
    Mohan, C. Nalini
    BALI MEDICAL JOURNAL, 2015, 4 (02) : 98 - 101