A giant choledochal cyst in a 17 year old female managed in a resource limited setting: A case report

被引:2
作者
Atwine, Oscar [1 ]
Odongo, Charles Newton [2 ,3 ]
Ainomugisha, Racheal [1 ]
Tayebwa, Edson [1 ]
Muhumuza, Joshua [4 ,5 ]
Dreque, Carlos Cabrera [1 ]
机构
[1] Mbarara Univ Sci & Technol, Fac Med, Dept Surg, Mbarara, Uganda
[2] Soroti Univ, Fac Med, Dept Anat, Soroti, Uganda
[3] Mbarara Univ Sci & Technol, Fac Med, Dept Surg, Div Pediat Surg, Mbarara, Uganda
[4] Kampala Int Univ, Fac Clin Med & Dent, Dept Surg, Western Campus, Bushenyi, Uganda
[5] Mubende Reg Referral Hosp, Dept Surg, Mubende, Uganda
关键词
Giant choledochal cyst; Resource limited setting; Case report; CHILDREN;
D O I
10.1016/j.ijscr.2023.108284
中图分类号
R61 [外科手术学];
学科分类号
摘要
Introduction and importance: Choledochal cysts are rare congenital bile duct anomalies that lead to cystic di-latations of the biliary tree. This condition is very rare in Africa. When these cysts exceed 10 cm in diameter, they are referred to as giant choledochal cysts, which are much rarer. Giant choledochal cysts present both a diag-nostic and surgical challenge. We present a case of a giant Choledochal cyst surgically managed in a resource limited setting with excellent outcome.Case presentation: A 17-year-old female presented with 4 months history of progressive abdominal distension associated with abdominal pain, yellow discoloration of eyes, and occasional constipation. Abdominal CT-scan revealed a huge cystic mass in the right upper quadrant extending inferiorly to the right lumbar region. Com-plete excision of a type IA choledochal cyst was done plus cholecystectomy in addition to bilioenteric recon-struction. The patient recovered uneventfully.Discussion and conclusion: To the best of our knowledge, this is the largest giant Choledochal cyst reported in literature. Even in a resource limited settings, sonography and a CT scan may be all that is required to make a diagnosis. During surgical excision, the surgeon should take extra caution to carefully dissect the adhesions off the giant cyst for a successful complete excision.
引用
收藏
页数:5
相关论文
共 15 条
[1]   The SCARE 2018 statement: Updating consensus Surgical CAse REport (SCARE) guidelines [J].
Agha, Riaz A. ;
Borrelli, Mimi R. ;
Farwana, Reem ;
Koshy, Kiron ;
Fowler, Alexander J. ;
Orgill, Dennis P. ;
Zhu, Hongyi ;
Alsawadi, Abdulrahman ;
Noureldin, Ashraf ;
Rao, Ashwini ;
Enam, Ather ;
Thoma, Achilleas ;
Bashashati, Mohammad ;
Vasudevan, Baskaran ;
Beamish, Andrew ;
Challacombe, Ben ;
De Wilde, Rudy Leon ;
Machado-Aranda, David ;
Laskin, Daniel ;
Muzumdar, Dattatraya ;
D'cruz, Anil ;
Manning, Todd ;
Healy, Donagh ;
Pagano, Duilio ;
Goel, Prabudh ;
Ranganathan, Priya ;
Pai, Prathamesh S. ;
Raja, Shahzad ;
Athe, M. Hammad ;
Kadioazlu, Huseyin ;
Nixon, Iain ;
Mukherjee, Indraneil ;
Gomez Riva, Juan ;
Raveendran, Kandiah ;
Derbyshire, Laura ;
Valmasoni, Michele ;
Chalkoo, Mushtaq ;
Raison, Nicholas ;
Muensterer, Oliver ;
Bradley, Patrick ;
Roberto, Coppola ;
Afifi, Raafat ;
Rosin, David ;
Klappenbach, Roberto ;
Wynn, Rolf ;
Giordano, Salvatore ;
Basu, Somprakas ;
Surani, Salim ;
Suman, Paritosh ;
Thorat, Mangesh .
INTERNATIONAL JOURNAL OF SURGERY, 2018, 60 :132-136
[2]  
ALONSO-LEJ F, 1959, Int Abstr Surg, V108, P1
[3]  
BABBITT DP, 1969, ANN RADIOL-RADIOL CL, V12, pR231
[4]  
Chaudhary A, 1996, BRIT J SURG, V83, P186, DOI 10.1002/bjs.1800830212
[5]   Transition of Techniques to Treat Choledochal Cysts in Children [J].
Dalton, Brian G. A. ;
Gonzalez, Katherine W. ;
Dehmer, Jeffrey J. ;
Andrews, Walter S. ;
Hendrickson, Richard J. .
JOURNAL OF LAPAROENDOSCOPIC & ADVANCED SURGICAL TECHNIQUES, 2016, 26 (01) :62-65
[6]   Choledochal malformations in adults in the Netherlands: Results from a nationwide retrospective cohort study [J].
de Kleine, Ruben H. ;
Schreuder, A. Marthe ;
ten Hove, Anneke ;
Hulscher, Jan B. F. ;
Rinkes, Inne H. M. Borel ;
Dejong, Cornelis H. C. ;
de Jonge, Jeroen ;
de Reuver, Philip ;
Erdmann, Joris ;
Kazemier, Geert ;
van Gulik, Thomas M. ;
Gouw, Annette S. H. ;
Porte, Robert J. .
LIVER INTERNATIONAL, 2020, 40 (10) :2469-2475
[7]  
Grover Shabnam Bhandari, 2022, Radiol Case Rep, V17, P404, DOI 10.1016/j.radcr.2021.10.051
[8]  
Khare Manish Kumar, 2015, Trop Gastroenterol, V36, P120
[9]   Choledochal cyst Todani IA case report [J].
Lira, Ana Karen Medina ;
Soto, Argenis Jose Mayorga ;
Frigerio, Pamela .
INTERNATIONAL JOURNAL OF SURGERY CASE REPORTS, 2016, 28 :293-295
[10]  
Miyano Takeshi, 1997, Current Opinion in Pediatrics, V9, P283, DOI 10.1097/00008480-199706000-00018