Two Very Rare Cases of Metastatic Thymic Carcinoma with Sjogren's Syndrome: A Case Series

被引:0
作者
Smith, Amy E. [1 ,2 ]
Kane, Alisa [3 ,4 ]
Watts, Francesca [5 ]
Qiu, Min [2 ,5 ,6 ]
Chin, Venessa [1 ,4 ,7 ]
机构
[1] St Vincents Hosp, Kinghorn Canc Ctr, Sydney, NSW, Australia
[2] Univ Notre Dame Australia, Sch Med, Sydney, NSW, Australia
[3] St Vincents Hosp, Dept Immunol & HIV, Sydney, NSW, Australia
[4] Univ New South Wales, Sch Med & Hlth, Sydney, NSW, Australia
[5] St Vincents Hosp, Dept Anat Pathol, Sydney, NSW, Australia
[6] St Vincents Hosp, SydPath, Sydney, NSW, Australia
[7] Garvan Institue Med Res, Sydney, NSW, Australia
关键词
Thymic carcinoma; Paraneoplastic syndrome; Sjogren's syndrome; Immunotherapy; Autoimmune disorder; PARANEOPLASTIC SYNDROMES; MULTICENTER; THYMOMA;
D O I
10.1159/000529425
中图分类号
R73 [肿瘤学];
学科分类号
100214 ;
摘要
Thymic tumours are rare thoracic malignancies with thymic carcinoma accounting for approximately 12% of all thymic tumours compared to thymomas which account for approximately 86%. Unlike thymomas, it is very rare for thymic carcinomas to be associated with autoimmune disorders or paraneoplastic syndromes. When these phenomena do occur, the vast majority are myasthenia gravis, pure red cell aplasia, or systemic lupus erythematous. Paraneoplastic Sjogren's syndrome is a rare complication of thymic carcinoma, with only two cases previously reported. Here we present 2 cases of patients with metastatic thymic carcinoma who developed autoimmune phenomena consistent with Sjogren's syndrome without classical symptoms prior to treatment. One patient opted for surveillance of their malignancy, while the other underwent chemoimmunotherapy with favourable results. These case reports describe two distinctive clinical presentations of a rare paraneoplastic phenomenon.
引用
收藏
页码:116 / 123
页数:8
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