Intensive physical training in children with heritable connective tissue disorders is feasible and safe: a pilot study

被引:0
作者
de Koning, Lisanne [1 ,2 ]
Warnink-Kavelaars, Jessica [2 ,3 ]
van Vulpen, Liesbeth [1 ,4 ]
van der Hulst, Annelies [5 ]
Rombaut, Lies [6 ]
van Meulenbroek, Thijs [7 ]
Oosterlaan, Jaap [8 ,9 ,10 ]
Rameckers, Eugene [11 ,12 ,13 ]
Engelbert, Raoul [1 ,2 ,3 ]
机构
[1] Amsterdam Univ Appl Sci, Fac Hlth, Ctr Expertise Urban Vital, Amsterdam, Netherlands
[2] Univ Amsterdam, Dept Rehabil Med, Amsterdam UMC Locat, Amsterdam, Netherlands
[3] Amsterdam Movement Sci Rehabil & Dev, Amsterdam, Netherlands
[4] Reade, Ctr Rehabil & Rheumatol, Amsterdam, Netherlands
[5] Univ Amsterdam, Emma Childrens Hosp, Dept Pediat Cardiol, Amsterdam UMC Locat, Amsterdam, Netherlands
[6] Univ Ghent, Ghent Univ Hosp, Ctr Med Genet, Ghent, Belgium
[7] Maastricht Univ, Res Sch CAPHRI, Dept Rehabil Med, Maastricht, Netherlands
[8] Univ Amsterdam, Emma Childrens Hosp, Dept Pediat, Amsterdam UMC Follow Me program, Amsterdam, Netherlands
[9] Univ Amsterdam, Emma Childrens Hosp, Emma Neurosci Grp, Amsterdam UMC locat, Amsterdam, Netherlands
[10] Amsterdam Reprod & Dev, Amsterdam, Netherlands
[11] Ghent Univ Hosp, Dept Phys & Rehabil Med Child Rehabil, Ghent, Belgium
[12] Adelante, Ctr Expertise Rehabil & Audiol, Hoensbroek, Netherlands
[13] UHasselt, Fac Rehabil Sci, Pediat Physiotherapy, REVAL, Hasselt, Belgium
关键词
Heritable connective tissue disorders; high intensity interval training; functional power training; physical fitness; pediatric physical therapy; COGNITIVE-BEHAVIORAL THERAPY; CHRONIC MUSCULOSKELETAL PAIN; EHLERS-DANLOS-SYNDROME; CLINICAL-SIGNIFICANCE; YOUNG-CHILDREN; HEALTH; ADOLESCENTS; REHABILITATION; HYPERMOBILITY; RELIABILITY;
D O I
10.1080/09638288.2025.2467772
中图分类号
R49 [康复医学];
学科分类号
100215 ;
摘要
PurposeThis pilot study assessed the feasibility, safety, and acceptability of a physical training program combined with parental meetings for children with heritable connective tissue disorders (HCTD), including Marfan syndrome (MFS), Loeys-Dietz syndrome (LDS), and Ehlers-Danlos syndromes (EDS). Secondary, it aimed to explore preliminary observations regarding the program's impact on individual training goals and physical fitness, including aerobic and anaerobic capacity, strength, agility, pain, fatigue, and disability.Materials and methodsThe intervention comprised functional power training (FPT) and high-intensity interval training (HIIT) conducted three times a week over 12 weeks. Data on feasibility, safety, and acceptability were collected, along with preliminary observations on physical fitness performance.ResultsThe intervention was feasible and safe, with no serious adverse events reported. However, acceptability was limited, with a participation rate of 27.8%. Preliminary findings revealed that 80% of participants achieved their training goals, 75% improved their aerobic capacity, and 70% showed gains in strength and agility, alongside reported reductions in pain and fatigue.ConclusionThis study highlights the potential benefits of tailored physical training for children with HCTD. Despite acceptability challenges, the intervention demonstrated feasibility and safety, providing a foundation for larger-scale effectiveness studies that include systematic feedback mechanisms to enhance participant engagement.
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页数:10
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